巨大囊性淋巴管瘤是婴儿急腹症的罕见病因:病例报告和文献综述。

Q4 Dentistry
Chrysovalantis Mariorakis, Eleni Boutouridou, Athanasios Pegios, Vasilki Magaliou, Marianna Polydoridou, Ioannis Georgakis, Elpis Chochliourou, Ilias Chatziioannidis, Elissavet Anestiadou, Georgios Papouis
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引用次数: 0

摘要

淋巴管瘤是一种源于淋巴的良性肿块,主要侵犯头颈部和口腔,腹部并不常见。临床表现由起源部位和大小决定。本病例是一名 10 个月大的男婴,既往无病史,因弥漫性腹痛和腹胀入院。体格检查发现左腹部有一个巨大的、可触及的肿块,腹部有压痛、畏缩和僵硬感。腹部超声波检查发现一个多球形、无法测量的肿块,有囊性和实性成分,提示为巨大囊性淋巴管瘤。患者接受了多载体计算机断层扫描和磁共振成像检查,以估计肿瘤的大小和延伸范围,从而制定术前计划。此外,甲胎蛋白水平升高进一步证实了肿瘤的肿瘤性来源。患者接受了探查性开腹手术,发现了一个大小约为 13.9×16.7×15.4 厘米的肿块,并在阴性边缘完全切除了肿瘤。组织病理结果证实了最初的诊断。患者术后恢复顺利,随访 6 个月未见复发迹象。婴儿腹部巨大淋巴管瘤极为罕见,密切关注并发症至关重要。完全切除的手术治疗被认为是最佳治疗方法。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Giant cystic lymphangioma as a rare cause of acute abdomen in infancy: a case report and literature review.

Lymphangioma, a benign mass of lymphatic origin, primarily affects the head, neck, and oral cavity, with the abdomen being an uncommon location. Clinical presentation is defined by site of origin and size. We present the case of a 10-month-old male infant with no previous medical history, admitted to our department with diffuse abdominal pain and distension. Physical examination revealed a huge, palpable mass arising from the left abdomen, abdominal tenderness, guarding, and rigidity. Abdominal ultrasound revealed a multilocular, non-measurable mass with both cystic and solid components that were suggestive of a giant cystic lymphangioma. Multidetector computed tomography and magnetic resonance imaging were performed to estimate the size and extension of the tumor for preoperative planning. Moreover, an elevated alpha-fetoprotein level further supported the neoplastic origin of the tumor. Exploratory laparotomy was performed, and a mass measuring approximately 13.9×16.7×15.4 cm was identified and completely excised in negative margins. Histopathological findings confirmed the initial diagnosis. Our patient had an uncomplicated postoperative course and recovery, with no signs of recurrence on a 6-month follow-up. Giant abdominal lymphangiomas in infants are extremely rare and close attention for complications is vital. Surgical intervention with complete resection is considered the optimal management.

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来源期刊
Folia medica
Folia medica Medicine-Medicine (all)
CiteScore
1.00
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0.00%
发文量
121
审稿时长
5 weeks
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