混合性性腺发育不良患者的单中心经验

IF 1.3 Q3 PEDIATRICS
Ebru Barsal Çetiner, Zeynep Donbaloğlu, Berna Singin, Bilge Aydın Behram, Kürşat Çetin, Güngör Karagüzel, Hale Tuhan, Mesut Parlak
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引用次数: 0

摘要

混合性性腺发育不良(MGD)是一种不常见的染色体性发育障碍(DSD)。有关其临床表现和生长模式的信息尚不充分。本研究旨在提供更多有关混合性性腺发育不良的信息,因为这种疾病尚未得到充分定义。研究人员回顾性审查了10名被诊断为混合性性腺发育不良患者的数据。对患者的临床表现、入院时的主诉、影像学检查、遗传学结果和接受的治疗进行了研究。多学科委员会决定对患者的性腺状态和性别进行饲养和评估。如果接受了生长激素治疗,则对治疗剂量和身高增长情况进行检查。患者入院时的年龄从 6 个月到 17.5 岁不等。患者的中位身高SDS为-0.75(2.73),平均体重SDS为-0.49(±1.46),平均体重指数(BMI)SDS为0.26(±0.97)。入院时的主诉各不相同,包括生殖器模糊、身材矮小和无月经。有些患者完全是女性表型,而有些则是男性化不足的男性表型。外部男性化评分(EMS)从 1 到 6.5 不等。多学科委员会决定将 6 名患者提升为女性,将 4 名患者提升为男性。被诊断为身材矮小的女性患者接受了生长激素治疗。接受治疗的患者的身高 SDS 增长率为 0.42(±0.49)。由于混合性性腺发育不良的罕见性和临床表现的多样性,我们对这种疾病的了解十分有限。因此,早期诊断和个体化治疗方案对这类患者至关重要。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Single-Center Experience in Patients with Mixed Gonadal Dysgenesis.

Mixed gonadal dysgenesis (MGD) is an uncommon chromosomal Disorder of Sexual Development (DSD). There is insufficient information regarding clinical findings and growth patterns. This study aimed to provide more information about mixed gonadal dysgenesis, which has not yet been sufficiently defined. Data from 10 patients diagnosed with mixed gonadal dysgenesis were retrospectively reviewed. Clinical presentations, complaints at admission, imaging, genetic results, and treatments received by the patients were examined. Gonadal status and the gender of the patients were reared and evaluated by a multidisciplinary council decision. If received, growth hormone treatment doses and height gains were examined. The patients' ages at admission range from 6 months to 17.5 years. The median height SDS of the patients was -0.75 (2.73), the mean body weight SDS was -0.49 (±1.46), and the mean body mass index (BMI) SDS was 0.26 (±0.97). The complaints at admission varied, including ambiguous genitalia, short stature, and absence of menstruation. Some patients are completely in the female phenotype, while some are inadequately virilized male phenotype. External Masculinization Score (EMS) ranges from 1 to 6.5. The decision to raise 6 patients as female and 4 patients as male was made by a multidisciplinary council. Growth hormone treatment was administered to patients raised as female and diagnosed with short stature. The height SDS gain in treated patients was 0.42 (±0.49). Due to its rarity and varied clinical presentation, our knowledge about mixed gonadal dysgenesis is limited. Therefore, early diagnosis and individualized treatment plans are crucial for this patient group.

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