利用新一代测序技术识别真菌病的致病变体。

IF 0.6 4区 医学 Q4 HEMATOLOGY
Sunaina Shrestha, Kimberly Newsom, Joanna Melody Chaffin, Robert P Seifert
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引用次数: 0

摘要

真菌病(MF)是皮肤 T 细胞淋巴瘤(CTCL)的主要形式,由于其临床和组织学特征与良性皮肤病相似,给诊断带来了挑战。延迟诊断会导致治疗延误,这促使人们探索先进的诊断工具。下一代测序(NGS)可通过识别 CTCL 常见但良性炎症性疾病不存在的致病变异来提高疾病检测水平。我们旨在讨论 CTCL 中的新型和常见致病变异,以提高 NGS 作为辅助诊断工具的效用。这项试验性研究利用(NGS)鉴定了 10 例 MF 的致病变异。病例的选择基于 PCR 证实的 T 细胞受体克隆性,并有足够的 DNA 用于 NGS。GatorSeq NGS Panel、Illumina NextSeq500 和 QIAGEN Clinical Insight QCI 软件为测序、分析和变异解读提供了便利。NGS 发现了 8 个新的基因突变,包括 HLA-DRB1、AK2、ITPKB、HLA-B、TYRO3 和 CHD2。此外,还检测到了之前报道的 MF 相关基因突变,如 DNMT3A、STAT5B 和 SOCS1(仅小鼠研究)。检测到的变异涉及细胞凋亡、NF-kB、JAK-STAT 和 TCR 信号通路,为了解 MF 的发病机制提供了线索。研究还注意到 APC、AK2、TYRO3 和 ITPKB 等调控肿瘤增殖和凋亡的基因发生了突变。MF 病例与 HLA 基因突变有关。NGS 可提高 MF 的诊断率,因为检测致病变异,尤其是已知发生在 MF 中的致病变异,有利于肿瘤诊断而非炎症诊断。继续开展这项工作可能会发现治疗靶点。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Pathogenic variants of mycosis fungoides identified using next-generation sequencing.

Mycosis fungoides (MF), the predominant form of cutaneous T-cell lymphoma (CTCL), poses diagnostic challenges due to its clinical and histological resemblance to benign skin disorders. Delayed diagnosis contributes to therapeutic delays, prompting exploration of advanced diagnostics tools. Next-generation sequencing (NGS) may enhance disease detection by identifying pathogenic variants common to CTCL but absent in benign inflammatory disorders. We aim to discuss novel and common pathogenic variants in CTCL to enhance the utility of NGS as a diagnostic adjunct. This pilot study employed (NGS) to identify pathogenic variants in 10 MF cases. Cases were selected based on PCR-confirmed T-cell receptor clonality, with adequate DNA for NGS. GatorSeq NGS Panel, Illumina NextSeq500, and QIAGEN Clinical Insight QCI software facilitated sequencing, analysis, and variant interpretation. NGS revealed eight novel mutations in genes including HLA-DRB1, AK2, ITPKB, HLA-B, TYRO3, and CHD2. Additionally, previously reported MF-associated mutations such as DNMT3A, STAT5B, and SOCS1 (mouse study only) were detected as well. Detected variants were involved in apoptotic, NF-kB, JAK-STAT, and TCR signaling pathways, providing insights into MF pathogenesis. Mutations in genes like APC, AK2, TYRO3, and ITPKB that regulate tumor proliferation and apoptosis were noted. MF cases were associated with HLA gene mutations. NGS may enhance MF diagnosis, as the detection of pathogenic variants, particularly those known to occur in MF, favors a neoplastic diagnosis over an inflammatory diagnosis. Continuing this work may lead to the discovery of therapeutic targets.

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来源期刊
Journal of Hematopathology
Journal of Hematopathology HEMATOLOGYPATHOLOGY-PATHOLOGY
CiteScore
0.80
自引率
0.00%
发文量
45
期刊介绍: The Journal of Hematopathology aims at providing pathologists with a special interest in hematopathology with all the information needed to perform modern pathology in evaluating lymphoid tissues and bone marrow. To this end the journal publishes reviews, editorials, comments, original papers, guidelines and protocols, papers on ancillary techniques, and occasional case reports in the fields of the pathology, molecular biology, and clinical features of diseases of the hematopoietic system. The journal is the unique reference point for all pathologists with an interest in hematopathology. Molecular biologists involved in the expanding field of molecular diagnostics and research on lymphomas and leukemia benefit from the journal, too. Furthermore, the journal is of major interest for hematologists dealing with patients suffering from lymphomas, leukemias, and other diseases. The journal is unique in its true international character. Especially in the field of hematopathology it is clear that there are huge geographical variations in incidence of diseases. This is not only locally relevant, but due to globalization, relevant for all those involved in the management of patients.
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