特发性嗜睡症的诊断难题和负担:系统性文献综述。

Talia Boulanger, Pascale Pigeon, Stephen Crawford
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引用次数: 0

摘要

特发性嗜睡症(IH)是一种罕见的神经性睡眠障碍,其特点是尽管睡眠时间正常,但白天过度嗜睡,会严重影响患者的生活。特发性嗜睡症带来的负担不仅仅是白天过度嗜睡,它还会影响日常生活的方方面面。嗜睡症的特征性症状包括睡眠惰性/醉酒、睡眠时间长和日间认知功能障碍。本系统性综述评估了目前有关 IH 诊断难题和疾病负担的知识。在MEDLINE、Embase、Cochrane、灰色文献(诊断标准和治疗指南)、会议(2019-2022年)和临床试验数据库中检索了2012年至2022年期间发表的与IH相关的原始流行病学、临床、人文或经济学研究文献,共检索到97篇文章。研究结果表明,IH仍然是一种定义不清的排除性诊断,由于症状重叠和客观检测的不足,很难与2型嗜睡症区分开来。因此,IH 患者的诊断延迟时间长达 9 年。IH 所造成的经济负担还没有明显的特征。药物治疗可改善症状和功能状态,但很少能恢复正常的功能水平。这些发现凸显了对嗜睡中枢性疾病重新分类的必要性。现在,研究小组之间需要进一步合作,以确定和验证客观标记物,帮助重新定义嗜睡症的诊断标准。这将使IH从未来的靶向治疗干预中获益。这项研究由武田开发中心美洲公司(Takeda Development Center Americas, Inc.
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Diagnostic challenges and burden of idiopathic hypersomnia: a systematic literature review.

Idiopathic hypersomnia (IH) is a rare neurological sleep disorder, characterized by excessive daytime sleepiness despite normal sleep duration, that can significantly impact patient's lives. The burden of IH goes beyond excessive daytime sleepiness, pervading all aspects of everyday life. Characteristic and burdensome symptoms of IH include sleep inertia/drunkenness, long sleep duration, and daytime cognitive dysfunction. This systematic review assessed current knowledge regarding IH diagnostic challenges and burden of illness. Literature searches for original epidemiological, clinical, humanistic, or economic research relevant to IH published between 2012 and 2022 in MEDLINE, Embase, Cochrane, gray literature (diagnostic criteria and treatment guidelines), conferences (2019-2022), and clinical trial databases yielded 97 articles. Findings indicate that IH remains a poorly defined diagnosis of exclusion that is difficult to distinguish from narcolepsy type 2 because of symptom overlap and inadequacies of objective testing. Consequently, individuals with IH endure diagnostic delays of up to 9 years. The economic burden of IH has not been characterized to any appreciable extent. Pharmacological treatment options can improve symptoms and functional status, but rarely restores normal levels of functioning. These findings highlight the need to reclassify central disorders of hypersomnolence. Further collaboration is now required between research groups to identify and validate objective markers to help redefine diagnostic criteria for IH. This would move IH into a position that could benefit from future targeted therapeutic interventions. The study was funded by Takeda Development Center Americas, Inc.

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