首次报告科特迪瓦一个家族因 GJB2 复合杂合变异而导致非综合征性听力损失。

IF 1 4区 生物学 Q4 GENETICS & HEREDITY
Madoussou Toure, Ghita Amalou, Imane Ait Raise, N'kan Max Ange Mobio, Abderrahim Malki, Abdelhamid Barakat
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引用次数: 0

摘要

先天性听力损失的主要病因是遗传因素,其中 GJB2 被确定为不同种族群体的关键基因。此外,非综合征性听力损失主要是常染色体隐性遗传。我们使用桑格测序法分析了来自象牙海岸 13 个无血缘关系家庭的 17 名聋儿的 GJB2 基因。其中一个家庭的两个孩子患有严重的先天性耳聋,并表现出致病性复合杂合变异。这些变异包括无义替换(c.132G > A 或 p.Trp44Ter)和新发现的 7 个碱基对的重复(c.205_211dupTTCCCCA 或 p.Ser72ProfsTer32)。分离测试证实了这些变异,这是首次在科特迪瓦先天性听力损失家族中发现 GJB2。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
First report of an Ivorian family with nonsyndromic hearing loss caused by GJB2 compound heterozygous variants.

The primary etiology of congenital hearing loss is attributed to genetic factors, with GJB2 identified as a pivotal gene across diverse ethnic groups. Additionally, nonsyndromic hearing loss is predominantly inherited in an autosomal recessive manner. We used Sanger sequencing to analyze GJB2 in 17 deaf children from 13 unrelated Ivory Coast families. One family had two children born with severe congenital deafness and exhibited pathogenic compound heterozygous variants. These variants included a nonsense substitution (c.132G > A or p.Trp44Ter) and a newly discovered duplication of 7 base pairs (c.205_211dupTTCCCCA or p.Ser72ProfsTer32). Segregation testing confirmed these variants, marking the first identification of GJB2 in an Ivorian family with congenital hearing loss.

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来源期刊
Annals of Human Genetics
Annals of Human Genetics 生物-遗传学
CiteScore
4.20
自引率
0.00%
发文量
34
审稿时长
3 months
期刊介绍: Annals of Human Genetics publishes material directly concerned with human genetics or the application of scientific principles and techniques to any aspect of human inheritance. Papers that describe work on other species that may be relevant to human genetics will also be considered. Mathematical models should include examples of application to data where possible. Authors are welcome to submit Supporting Information, such as data sets or additional figures or tables, that will not be published in the print edition of the journal, but which will be viewable via the online edition and stored on the website.
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