Hojjat Naderi-Meshkin, Wiwit A Wahyu Setyaningsih, Andrew Yacoub, Garrett Carney, Victoria A Cornelius, Clare-Ann Nelson, Sophia Kelaini, Clare Donaghy, Philip D Dunne, Raheleh Amirkhah, Anna Zampetaki, Lingfang Zeng, Alan W Stitt, Noemi Lois, David J Grieve, Andriana Margariti
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DB-VOs display elevated levels of reactive oxygen species (ROS), heightened mitochondrial content and activity, increased proinflammatory cytokines, and reduced blood perfusion recovery in vivo. Through comprehensive single-cell RNA sequencing, we uncover molecular and functional differences, as well as signaling networks, between vascular cell types and clusters within DB-VOs. Our analysis identifies major vascular cell types (endothelial cells [ECs], pericytes, and vascular smooth muscle cells) within VOs, highlighting the dichotomy between ECs and mural cells. We also demonstrate the potential need for additional inductions using organ-specific differentiation factors to promote organ-specific identity in VOs. Furthermore, we observe basal heterogeneity within VOs and significant differences between DB-VOs and ND-VOs. 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引用次数: 0
摘要
由诱导多能干细胞(iPSC)衍生的血管器官(VO)有望成为体外疾病模型和药物筛选平台。然而,它们忠实再现人类血管疾病和细胞组成的能力仍不清楚。在本研究中,我们证明了与非糖尿病 VOs(ND-VOs)相比,由糖尿病供体的 iPSCs 衍生的 VOs(DB-VOs)表现出受损的血管功能。DB-VOs显示活性氧(ROS)水平升高、线粒体含量和活性增加、促炎细胞因子增加以及体内血液灌注恢复能力下降。通过全面的单细胞 RNA 测序,我们发现了 DB-VOs 中血管细胞类型和细胞簇之间的分子和功能差异以及信号网络。我们的分析确定了VOs内的主要血管细胞类型(内皮细胞、周细胞和血管平滑肌细胞),突出了内皮细胞和壁细胞之间的二分法。我们还证明,可能需要使用器官特异性分化因子进行额外诱导,以促进 VOs 中器官特异性特征的形成。此外,我们还观察到 VOs 内部的基础异质性以及 DB-VOs 和 ND-VOs 之间的显著差异。值得注意的是,我们发现了 DB-VOs 特异的 ECs 亚群,它们在 ROS 通路中的代表性过高,而在血管生成标志中的代表性过低,这表明糖尿病患者的血管生成出现异常。我们的研究结果强调了 VOs 在模拟糖尿病血管病变方面的潜力,强调了研究 VOs 内细胞异质性对疾病建模和药物发现的重要性,并提供了 ECs(尤其是 DB-VOs 中的 ECs)中 GAP43(神经调节蛋白)表达的证据,这对血管发育和疾病具有重要意义。
Unveiling impaired vascular function and cellular heterogeneity in diabetic donor-derived vascular organoids.
Vascular organoids (VOs), derived from induced pluripotent stem cells (iPSCs), hold promise as in vitro disease models and drug screening platforms. However, their ability to faithfully recapitulate human vascular disease and cellular composition remains unclear. In this study, we demonstrate that VOs derived from iPSCs of donors with diabetes (DB-VOs) exhibit impaired vascular function compared to non-diabetic VOs (ND-VOs). DB-VOs display elevated levels of reactive oxygen species (ROS), heightened mitochondrial content and activity, increased proinflammatory cytokines, and reduced blood perfusion recovery in vivo. Through comprehensive single-cell RNA sequencing, we uncover molecular and functional differences, as well as signaling networks, between vascular cell types and clusters within DB-VOs. Our analysis identifies major vascular cell types (endothelial cells [ECs], pericytes, and vascular smooth muscle cells) within VOs, highlighting the dichotomy between ECs and mural cells. We also demonstrate the potential need for additional inductions using organ-specific differentiation factors to promote organ-specific identity in VOs. Furthermore, we observe basal heterogeneity within VOs and significant differences between DB-VOs and ND-VOs. Notably, we identify a subpopulation of ECs specific to DB-VOs, showing overrepresentation in the ROS pathway and underrepresentation in the angiogenesis hallmark, indicating signs of aberrant angiogenesis in diabetes. Our findings underscore the potential of VOs for modeling diabetic vasculopathy, emphasize the importance of investigating cellular heterogeneity within VOs for disease modeling and drug discovery, and provide evidence of GAP43 (neuromodulin) expression in ECs, particularly in DB-VOs, with implications for vascular development and disease.
期刊介绍:
STEM CELLS, a peer reviewed journal published monthly, provides a forum for prompt publication of original investigative papers and concise reviews. STEM CELLS is read and written by clinical and basic scientists whose expertise encompasses the rapidly expanding fields of stem and progenitor cell biology.
STEM CELLS covers:
Cancer Stem Cells,
Embryonic Stem Cells/Induced Pluripotent Stem (iPS) Cells,
Regenerative Medicine,
Stem Cell Technology: Epigenetics, Genomics, Proteomics, and Metabonomics,
Tissue-Specific Stem Cells,
Translational and Clinical Research.