齿侧苍白球萎缩:癫痫、共济失调和舞蹈症的罕见病因。

IF 2.4 Q2 CLINICAL NEUROLOGY
Karthik Harisankar, Jagdeep Singh, Sahil Mehta, Vivek Lal
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引用次数: 0

摘要

一名 34 岁的妇女隐匿起病,10 年来小脑共济失调逐渐加重,并伴有全身抽搐。经检查,她有肌阵挛抽搐、舞蹈样运动和小脑综合征。她的家族史表明,该病为常染色体显性遗传。通过对三核苷酸重复疾病的遗传学分析,诊断结果为齿状突眼-苍白球萎缩症(atrophin-1基因中有60个CAG重复)。这种罕见的脊髓小脑共济失调症如合并癫痫发作和舞蹈症,应在遗传性共济失调症的鉴别诊断中予以考虑。其他提示重复扩增性疾病的特征是同一家族中的表型多变和可能的预期性。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Dentatorubral-pallidoluysian atrophy: a rare cause of epilepsy, ataxia and chorea.

A 34-year-old woman presented with insidious onset and gradually progressive cerebellar ataxia over 10 years, with generalised convulsions. On examination, there were myoclonic jerks, choreiform movements and cerebellar syndrome. Her family history suggested an autosomal dominant inheritance with anticipation. Genetic analysis for trinucleotide repeat disorders led to a diagnosis of dentatorubral-pallidoluysian atrophy (60 CAG repeats in the atrophin-1 gene). This rare spinocerebellar ataxia should be considered in the differential diagnosis of inherited ataxia when combined with seizures and chorea. Other features suggesting a repeat expansion disorder are variable phenotypes within the same family and possible anticipation.

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来源期刊
PRACTICAL NEUROLOGY
PRACTICAL NEUROLOGY Medicine-Neurology (clinical)
CiteScore
3.70
自引率
3.60%
发文量
113
期刊介绍: The essential point of Practical Neurology is that it is practical in the sense of being useful for everyone who sees neurological patients and who wants to keep up to date, and safe, in managing them. In other words this is a journal for jobbing neurologists - which most of us are for at least part of our time - who plough through the tension headaches and funny turns week in and week out. Primary research literature potentially relevant to routine clinical practice is far too much for any neurologist to read, let alone understand, critically appraise and assimilate. Therefore, if research is to influence clinical practice appropriately and quickly it has to be digested and provided to neurologists in an informative and convenient way.
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