由 CYP21A2 基因突变引起的 46XX 染色体男性先天性肾上腺皮质增生症的性别认同差异。

Pub Date : 2024-04-01 Epub Date: 2024-05-24 DOI:10.4103/ijabmr.ijabmr_473_23
K C Pradheep Kumar, Suranjana Banik, Praisy Joy, Sanjukta Sahoo
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引用次数: 0

摘要

一名二十多岁的男性患者因生殖器发育不全到我们的三级专科就诊,主诉是身材矮小和交配不足。他没有近亲结婚史,体检结果令人担忧他可能患有性发育障碍(DSD)。核型分析和荧光原位杂交结果显示,该患者存在两条X染色体,属于基因型女性。桑格测序显示,CYP21A2基因存在杂合致病突变,而该基因与21-羟化酶缺乏症有关,因此确诊为先天性肾上腺皮质增生症(CAH),Prader V期。细胞遗传学和分子遗传学研究在诊断和决策中起着至关重要的作用,发展中国家应负担得起这些研究,以更好地照顾患者。
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Divergent Gender Identity in a Phenotypic Male with 46XX Karyotype Caused by a Mutation in CYP21A2 Gene with Congenital Adrenal Hyperplasia.

A male patient in his late twenties presented with ambiguous genitalia to our tertiary specialist unit with complaints of short stature and inadequate copulation. There was no history of consanguinity, and a physical examination raised concerns about possible disorders of sexual development (DSD). Karyotyping and fluorescence in situ hybridization results were consistent with the presence of two X chromosomes, revealing the patient to be a genotypic female. Sanger sequencing showed a heterozygous pathogenic mutation in the CYP21A2 gene known to be associated with 21-hydroxylase deficiency, thus confirming the diagnosis of congenital adrenal hyperplasia (CAH), Prader stage V. DSD with CAH is distressing for the patient and their families, and the management needs a multidimensional approach involving diverse medical, genetic, and psychological considerations. Cytogenetic and molecular genetic studies play an essential role in diagnosis and decision-making and should be made affordable in developing countries for better patient care.

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