MYH9 相关疾病,唯一表现为终末期肾病,活体肾移植后长期无复发:病例报告。

IF 1 Q4 UROLOGY & NEPHROLOGY
Yuki Horibe, Kazuaki Yamanaka, Junya Kaimori, Yuji Miyata, Shota Fukae, Takahiro Yoshida, Masahiro Nakagawa, Yasuki Ishihara, Miho Nagata, Yohei Miyashita, Yoshihiro Asano, Hidefumi Kishikawa
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引用次数: 0

摘要

MYH9 相关疾病是一组由 MYH9 基因突变引起的常染色体显性遗传疾病,以血小板减少、感音神经性听力损失、白内障和肾功能衰竭为特征。在此,我们报告了一例因 MYH9 相关疾病导致慢性肾衰竭并伴有肾脏症状而接受活体肾移植的患者。患者在 12 岁时的一次体检中被诊断出患有蛋白尿。她的肾功能逐渐恶化,34 岁时开始接受血液透析。肾活检未明确诊断出肾病。35 岁时,她接受了以母亲为供体的活体肾移植手术。移植六年后,她的肾功能保持稳定,肾活检也没有发现复发性肾炎的迹象。家族病史显示,她的父亲、叔叔和弟弟都患有终末期肾病。基因检测发现了一个与 MYH9 基因有关的突变(p.E1653D)。由于她的父亲曾做过肾活检,并被诊断为局灶节段性肾小球硬化症(FSGS),因此我们诊断为与 MYH9 基因紊乱相关的 FSGS 导致的慢性肾衰竭。受试者及其患有肾衰竭的家庭成员中没有发现提示听力损失、白内障或血小板减少的病例,也没有发现肾衰竭以外的其他症状。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
MYH9-related disorder with sole presentation of end-stage kidney disease and long-term, recurrence-free living after living donor renal transplantation: a case report.

MYH9-related disorders are a group of autosomal dominant disorders caused by mutations in MYH9, and are characterized by thrombocytopenia, sensorineural hearing loss, cataracts, and renal failure. Here, we report a case of chronic renal failure due to MYH9-related disorder with renal symptoms in a patient who underwent living-donor renal transplantation. The patient was diagnosed with proteinuria during a health checkup at the age of 12 years. Her renal function gradually deteriorated, and hemodialysis was initiated at 34 years of age. No definitive diagnosis of renal disease was made through renal biopsy. At the age of 35, she underwent living-donor renal transplantation from her mother as the donor. Six years after transplantation, her renal function remained stable, and no evidence of recurrent nephritis was found during renal biopsies. The family history revealed that her father, uncle, and younger brother had end-stage kidney disease. Genetic testing revealed a mutation (p.E1653D) related to the MYH9 gene. As her father had a history of renal biopsy and was diagnosed with focal segmental glomerulosclerosis (FSGS), we diagnosed chronic renal failure due to FSGS associated with MYH9 disorder. There were no findings suggestive of hearing loss, cataracts, or thrombocytopenia in the recipient or their family members with renal failure, and no symptoms other than renal failure were noted.

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来源期刊
CEN Case Reports
CEN Case Reports UROLOGY & NEPHROLOGY-
CiteScore
1.90
自引率
0.00%
发文量
80
期刊介绍: Clinical and Experimental Nephrology (CEN) Case Reports is a peer-reviewed online-only journal, officially published biannually by the Japanese Society of Nephrology (JSN).  The journal publishes original case reports in nephrology and related areas.  The purpose of CEN Case Reports is to provide clinicians and researchers with a forum in which to disseminate their personal experience to a wide readership and to review interesting cases encountered by colleagues all over the world, from whom contributions are welcomed.
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