类似韦尼克脑病的神经脊髓炎谱系障碍:病例报告与文献综述。

IF 0.9 Q4 CLINICAL NEUROLOGY
Neurohospitalist Pub Date : 2024-04-01 Epub Date: 2024-01-16 DOI:10.1177/19418744241228004
Sloan Lynch, Nil Saez Calveras, Anik Amin
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引用次数: 0

摘要

我们描述了一例模仿韦尼克脑病(WE)的神经脊髓炎视网膜频谱紊乱症(NMOSD)病例,以突出 NMOSD 的非典型表现。一名 39 岁女性出现亚急性脑病和进行性眼球震颤。她的核磁共振成像显示,乳腺体、丘脑周围灰质、丘脑内侧、第三脑室和脑后区均出现T2高密度。全血硫胺素水平升高,静脉注射硫胺素也没有改善。脑脊液中淋巴细胞增多,蛋白质升高。她的血清 Aquaporin-4 (AQP4) 抗体检测呈阳性。随后的影像学检查发现颈椎和胸椎脊髓有多层次病变。她的 CSF GFAP 抗体也呈阳性。经过大剂量静脉注射类固醇和血浆置换术后,她的病情稳步明显好转。后来,她开始接受利妥昔单抗的慢性治疗。这是一例独特的 NMOSD 病例,她具有 WE 的典型临床和影像学特征,而非 NMOSD 的典型症状。因此,当担心出现间脑和中线病变时,应考虑脱髓鞘疾病,尤其是在没有典型 WE 危险因素的情况下。反之,临床医生也应注意严重脑后区综合征引起的继发性营养并发症。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Neuromyelitis Optica Spectrum Disorder Resembling Wernicke's Encephalopathy: A Case Report and Review of the Literature.

We describe a case of Neuromyelitis Optica Spectrum Disorder (NMOSD) mimicking Wernicke's Encephalopathy (WE) to highlight an atypical presentation of NMOSD. A 39-year-old female presented with subacute encephalopathy and progressive ophthalmoplegia. Her MRI revealed T2 hyperintensities involving the mammillary bodies, periaqueductal grey matter, medial thalami, third ventricle, and area postrema. Whole blood thiamine levels were elevated and she did not improve with IV thiamine. CSF was notable for lymphocytic pleocytosis and elevated protein. She tested positive for serum Aquaporin-4 (AQP4) antibody. Subsequent imaging revealed multilevel lesions in the cervical and thoracic spinal cord. Her CSF GFAP antibody also came back positive. She steadily and significantly improved after high-dose IV steroids and plasmapheresis. She later started on chronic rituximab therapy. This represents a unique case of NMOSD presenting with the classical clinical and imaging features of WE, as opposed to the typical presenting symptoms of NMOSD. As such, demyelinating disorders should be considered when there is concern for diencephalic and midline pathologies, particularly without classic WE risk factors. Conversely, clinicians should be aware of secondary nutritional complications arising from severe area postrema syndrome.

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来源期刊
Neurohospitalist
Neurohospitalist CLINICAL NEUROLOGY-
CiteScore
1.60
自引率
0.00%
发文量
108
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