戈谢病:印度尼西亚首例成人病例。

IF 0.7 Q3 MEDICINE, GENERAL & INTERNAL
Acta medica Indonesiana Pub Date : 2024-01-01
Ardhi Rahman Ahani, Cosphiadi Irawan, Agnes Stephanie Harahap, Klara Yuliarti, Maria Francisca Ham, Faramitha Nur Izzaty, Damayanti Rusli Sjarif
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引用次数: 0

摘要

一名 44 岁的女性因腹部胀痛和乏力前来就诊。体格检查时发现脾脏肿大。实验室检查发现全血细胞减少,白蛋白-球蛋白比值下降。腹部超声波检查显示脾脏肿大、胆石症和膀胱炎,骨质检查显示骨质疏松。鉴别诊断包括白血病、多发性骨髓瘤和骨髓纤维化,因此进行了骨髓穿刺。然而,组织病理学检查在骨髓穿刺中发现了高雪氏样细胞。通过免疫组化染色,发现戈谢样细胞中的 CD68 呈阳性,支持戈谢病。为了确诊,对患者血浆中的葡萄糖苷底物进行了检查。葡萄糖酰鞘氨醇,一种葡萄糖基甘油酰胺的脱乙酰形式,明显升高。因此,确诊为戈谢病。这是印度尼西亚报告的首例成人戈谢病诊断病例。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Gaucher Disease: A First Reported Adult Case in Indonesia.

A 44-year-old female presented with a distended abdomen and fatigue. On physical examination, prominent splenomegaly was found. The laboratory investigations revealed pancytopenia and decreased albumin-globulin ratio. The abdominal ultrasonography revealed splenomegaly, cholelithiasis, and cystitis, and the bone survey showed osteopenia. Differential diagnoses included leukemia, multiple myeloma, and myelofibrosis therefore bone marrow puncture was performed. However, histopathologic examination found Gaucher-like cells in the bone marrow aspiration. The finding of CD68 positivity in Gaucher-like cells by using the immunohistochemistry staining supporting Gaucher disease. To confirm the diagnosis, an examination of glucocerebroside substrate from the patient's blood plasma was performed. Glucosylsphingosine, a deacylated form of glucosylceramide, was markedly elevated. Therefore, the diagnosis of Gaucher disease was confirmed. This is the first reported adult Gaucher case diagnosed in Indonesia.

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来源期刊
Acta medica Indonesiana
Acta medica Indonesiana MEDICINE, GENERAL & INTERNAL-
CiteScore
2.30
自引率
0.00%
发文量
61
审稿时长
12 weeks
期刊介绍: Acta Medica Indonesiana – The Indonesian Journal of Internal Medicine is an open accessed online journal and comprehensive peer-reviewed medical journal published by the Indonesian Society of Internal Medicine since 1968. Our main mission is to encourage the novel and important science in the clinical area in internal medicine. We welcome authors for original articles (research), review articles, interesting case reports, special articles, clinical practices, and medical illustrations that focus on the clinical area of internal medicine. Subjects suitable for publication include, but are not limited to the following fields of: -Allergy and immunology -Emergency medicine -Cancer and stem cells -Cardiovascular -Endocrinology and Metabolism -Gastroenterology -Gerontology -Hematology -Hepatology -Tropical and Infectious Disease -Virology -Internal medicine -Psychosomatic -Pulmonology -Rheumatology -Renal and Hypertension -Thyroid
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