{"title":"肺朗格汉细胞组织囊肿病伴有双侧同时性气胸--病例报告","authors":"Sophie Buckley , Emily O'Reilly , Deirdre Doyle , Desmond Murphy","doi":"10.1016/j.rmcr.2024.101999","DOIUrl":null,"url":null,"abstract":"<div><p>We describe the case of a young male, with no significant medical history, who presented to the Emergency Department (ED) with severe respiratory compromise. He suffered a respiratory arrest shortly after presentation. An initial chest x-ray performed post intubation revealed bilateral pneumothoraces with evidence of abnormal underlying lungs. Through a series of investigations, he was diagnosed with Pulmonary Langerhans Cell Histocystosis. In this article, we outline the initial presentation, subsequent acute management and the clinical course pertaining to this man's presentation. We believe this is the first reported presentation of bilateral simultaneous pneumothoraces, with previously unknown Pulmonary Langerhans Cell histiocytosis (PLCH).</p></div>","PeriodicalId":51565,"journal":{"name":"Respiratory Medicine Case Reports","volume":null,"pages":null},"PeriodicalIF":0.8000,"publicationDate":"2024-01-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"https://www.sciencedirect.com/science/article/pii/S2213007124000224/pdfft?md5=65fcb9b58220331c1c889bcad1b1799b&pid=1-s2.0-S2213007124000224-main.pdf","citationCount":"0","resultStr":"{\"title\":\"Pulmonary Langerhan's cell histocystosis presenting with bilateral simultaneous pneumothoraces – Case report\",\"authors\":\"Sophie Buckley , Emily O'Reilly , Deirdre Doyle , Desmond Murphy\",\"doi\":\"10.1016/j.rmcr.2024.101999\",\"DOIUrl\":null,\"url\":null,\"abstract\":\"<div><p>We describe the case of a young male, with no significant medical history, who presented to the Emergency Department (ED) with severe respiratory compromise. He suffered a respiratory arrest shortly after presentation. An initial chest x-ray performed post intubation revealed bilateral pneumothoraces with evidence of abnormal underlying lungs. Through a series of investigations, he was diagnosed with Pulmonary Langerhans Cell Histocystosis. In this article, we outline the initial presentation, subsequent acute management and the clinical course pertaining to this man's presentation. We believe this is the first reported presentation of bilateral simultaneous pneumothoraces, with previously unknown Pulmonary Langerhans Cell histiocytosis (PLCH).</p></div>\",\"PeriodicalId\":51565,\"journal\":{\"name\":\"Respiratory Medicine Case Reports\",\"volume\":null,\"pages\":null},\"PeriodicalIF\":0.8000,\"publicationDate\":\"2024-01-01\",\"publicationTypes\":\"Journal Article\",\"fieldsOfStudy\":null,\"isOpenAccess\":false,\"openAccessPdf\":\"https://www.sciencedirect.com/science/article/pii/S2213007124000224/pdfft?md5=65fcb9b58220331c1c889bcad1b1799b&pid=1-s2.0-S2213007124000224-main.pdf\",\"citationCount\":\"0\",\"resultStr\":null,\"platform\":\"Semanticscholar\",\"paperid\":null,\"PeriodicalName\":\"Respiratory Medicine Case Reports\",\"FirstCategoryId\":\"1085\",\"ListUrlMain\":\"https://www.sciencedirect.com/science/article/pii/S2213007124000224\",\"RegionNum\":0,\"RegionCategory\":null,\"ArticlePicture\":[],\"TitleCN\":null,\"AbstractTextCN\":null,\"PMCID\":null,\"EPubDate\":\"\",\"PubModel\":\"\",\"JCR\":\"Q4\",\"JCRName\":\"RESPIRATORY SYSTEM\",\"Score\":null,\"Total\":0}","platform":"Semanticscholar","paperid":null,"PeriodicalName":"Respiratory Medicine Case Reports","FirstCategoryId":"1085","ListUrlMain":"https://www.sciencedirect.com/science/article/pii/S2213007124000224","RegionNum":0,"RegionCategory":null,"ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":null,"EPubDate":"","PubModel":"","JCR":"Q4","JCRName":"RESPIRATORY SYSTEM","Score":null,"Total":0}
引用次数: 0
摘要
我们描述了这样一例病例:一名年轻男性,无明显病史,因严重呼吸衰竭到急诊科就诊。他在就诊后不久呼吸骤停。插管后进行的初步胸部 X 光检查发现双侧气胸,并有肺部异常的迹象。通过一系列检查,他被诊断为肺朗格汉斯细胞组织囊肿。在本文中,我们将概述这名患者的最初表现、随后的急性处理和临床过程。我们认为,这是首次报道双侧同时出现气胸,且之前并不知晓肺朗格汉斯细胞组织细胞增生症(PLCH)的病例。
Pulmonary Langerhan's cell histocystosis presenting with bilateral simultaneous pneumothoraces – Case report
We describe the case of a young male, with no significant medical history, who presented to the Emergency Department (ED) with severe respiratory compromise. He suffered a respiratory arrest shortly after presentation. An initial chest x-ray performed post intubation revealed bilateral pneumothoraces with evidence of abnormal underlying lungs. Through a series of investigations, he was diagnosed with Pulmonary Langerhans Cell Histocystosis. In this article, we outline the initial presentation, subsequent acute management and the clinical course pertaining to this man's presentation. We believe this is the first reported presentation of bilateral simultaneous pneumothoraces, with previously unknown Pulmonary Langerhans Cell histiocytosis (PLCH).