2000 年代后 Kii 肌萎缩性脊髓侧索硬化症的持续存在及其与衰老相关的特征性 tau 星形胶质细胞病变。

IF 3.2 3区 医学 Q2 CLINICAL NEUROLOGY
Kazumi Tsuji, Yoshiaki Nakayama, Junko Taruya, Hidefumi Ito
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引用次数: 0

摘要

纪伊肌萎缩性脊髓侧索硬化症(ALS)是一种发生在纪伊半岛南部的独特疾病,表现出 TAR DNA 结合蛋白 43 kDa(TDP-43)蛋白病和牛磺酸蛋白病的双重病理特征。20 世纪 60 年代,该地区肌萎缩性脊髓侧索硬化症的发病率非常高,到 20 世纪 80 年代曾短暂下降,但 2000 年后,随着高发地域病灶的变化,发病率又开始上升。然而,目前还不清楚独特的病理特征是否随着发病率的变化而改变。本研究分析了 20 世纪 70 年代(4 例)和 1999 年以后(12 例)经神经病理学证实的纪伊肌萎缩性脊髓侧索硬化症病例的尸检标本,这些标本来自纪伊半岛南部或该地区以外。我们的研究结果证实,2000年后,Kii ALS继续在纪伊半岛南部发生,并保留了该病特有的神经元tau病理特征,包括广泛存在于整个大脑和脊髓、稀疏的神经髓丝、浅表层占主导地位等。此外,我们首次根据老化相关tau星形胶质细胞病变分类方法评估了纪伊和非纪伊ALS的胶质tau病变,发现纪伊ALS病例中灰质老化相关tau星形胶质细胞病变以脑干为主的独特表现,这可能为发病机制提供了线索。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Persistence of Kii amyotrophic lateral sclerosis after the 2000s and its characteristic aging-related tau astrogliopathy.

Kii amyotrophic lateral sclerosis (ALS) is a unique disease that occurs in the southern portion of the Kii Peninsula and exhibits a dual pathology of TAR DNA-binding protein of 43 kDa (TDP-43) proteinopathy and tauopathy. The incidence of ALS in this region was very high in the 1960s, briefly decreased through the 1980s, but began increasing again after 2000 with a change of high-concentration geographic foci. It is unclear, however, whether the unique pathological features have changed along with the incidence changes. This study analyzed postmortem specimens from neuropathologically confirmed Kii ALS cases from the 1970s (n = 4) and those after 1999 (n = 12) from the southern Kii Peninsula or outside of the area. Our results confirm the continued occurrence of Kii ALS after 2000 in the southern Kii Peninsula and the preservation of disease-specific neuronal tau pathology, including the widespread occurrence throughout the brain and spinal cord, sparse neuropil threads, and predominance in superficial layers. Furthermore, we assessed the glial tau pathology of Kii and non-Kii ALS in accordance with the aging-related tau astrogliopathy classification method for the first time and detected a unique brainstem predominant appearance of gray matter aging-related tau astrogliopathy in Kii ALS cases, which may provide clues to pathogenetic mechanisms.

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来源期刊
CiteScore
5.40
自引率
6.20%
发文量
118
审稿时长
6-12 weeks
期刊介绍: Journal of Neuropathology & Experimental Neurology is the official journal of the American Association of Neuropathologists, Inc. (AANP). The journal publishes peer-reviewed studies on neuropathology and experimental neuroscience, book reviews, letters, and Association news, covering a broad spectrum of fields in basic neuroscience with an emphasis on human neurological diseases. It is written by and for neuropathologists, neurologists, neurosurgeons, pathologists, psychiatrists, and basic neuroscientists from around the world. Publication has been continuous since 1942.
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