亨廷顿舞蹈症和大脑发育

Pub Date : 2022-12-08 DOI:10.5802/crbiol.93
Sandrine Humbert, Monia Barnat
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引用次数: 1

摘要

亨廷顿氏病是一种罕见的遗传性神经系统疾病,通常表现在轻度成年期。该疾病的特点是特定大脑结构的功能障碍和退化,逐渐导致精神、认知和运动障碍。这种疾病是由亨廷顿蛋白编码基因的突变引起的,尽管它出现在成年期,但胚胎在子宫内发育时就携带了突变的基因。基于小鼠模型和人类干细胞的研究报告了疾病条件下改变的发育机制。然而,这种突变会影响人类的发育吗?关注携带HD突变的人类胎儿大脑发育的早期阶段,我们已经确定了新皮层发育的异常,新皮层是确保大脑高级功能的结构。总之,这些研究表明,发育缺陷可能有助于成人的发病症状,改变对疾病的看法,从而改变患者的医疗保健。
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Huntington's disease and brain development.

Huntington's disease is a rare inherited neurological disorder that generally manifests in mild-adulthood. The disease is characterized by the dysfunction and the degeneration of specific brain structures leading progressively to psychiatric, cognitive and motor disorders. The disease is caused by a mutation in the gene coding for huntingtin and, although it appears in adulthood, embryos carry the mutated gene from their development in utero. Studies based on mouse models and human stem cells have reported altered developmental mechanisms in disease conditions. However, does the mutation affect development in humans? Focusing on the early stages of brain development in human fetuses carrying the HD mutation, we have identified abnormalities in the development of the neocortex, the structure that ensure higher cerebral functions. Altogether, these studies suggests that developmental defects could contribute to the onset symptoms in adults, changing the perspective on disease and thus the health care of patients.

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