P. Battepati, Priyanka Gupta, B. Manjunatha, B. S. Manasali
{"title":"Odontogenic Choriostoma in buccal mucosa associated with suspected Goldenhar Syndrome","authors":"P. Battepati, Priyanka Gupta, B. Manjunatha, B. S. Manasali","doi":"10.15761/icst.1000307","DOIUrl":null,"url":null,"abstract":"Presence of teeth or tooth like masses at unusual sites of perioral structures like maxillary sinus, nasal cavity, ear, lip etc have been occasionally reported. But presence of fully developed dental structures with supporting skeletal tissue at non tooth bearing areas is extremely rare entity. In this report a similar case of presence of supplemental dental tissue along with supporting skeletal structure at buccal mucosa affecting facial symmetry which was associated with suspected Goldenhar Syndrome is presented. Report of such condition is extremely scanty in available literature and has been termed as OdotogenicChoriostoma by certain authors. *Correspondence to: Manjunatha BS, Associate Professor, Department of Oral Biology, Chairman, Scientific Presentation Committee, Member, Examination Unit, Faculty of Dentistry, Taif University, Kingdom of Saudi Arabia, E-mail: drmanju26@hotmail.com Received: April 09, 2019; Accepted: April 25, 2019; Published: April 29, 2019 Background Presence of tooth or tooth like structures at extragingival sites is not uncommon. Various extra gingival sites are reported for presence of such kind of structures like nasal cavity, maxillary sinus, ear, tongue as well as mandibular condylar and coronoid process. Presence of such structures may cause malocclusion, difficulty in breathing, incomplete articulation and speech alteration. Some of them are diagnosed early whereas some remain subclinical and diagnosed incidentally on radiograph. Confirmatory diagnosis for such structures is made by co relating clinical, radiographic and histological examination. Presence of tooth like structures at unusual site is considered ectopic and their presence in soft tissue is seldom observed. The term ‘‘choriostoma’’ has been proposed for such kind of structures which are histologically normal for a part of body except at the site where it is located [1]. Primary classification of choriostoma has been proposed based on its clinical and histomorphologic features like salivary gland choriostoma, osseous and cartilaginous choriostoma, glial and gastric choriostoma etc [2]. Osseous and cartilageous types of choriostoma are most commonly seen in oral cavity [1]. For presentation of such lesions with dental component as well as its location on extra gingival site, term ‘odontogenic choriostoma’ seems to be appropriate. We present an unusual case of an 8 year old girl with presence of tooth like structures in right buccal mucosa with supporting bony extension from right maxillary posterior region associated with suspected case of Goldenhar syndrome, for which term odontogenic choriostoma is used.","PeriodicalId":90850,"journal":{"name":"Integrative cancer science and therapeutics","volume":"1 1","pages":""},"PeriodicalIF":0.0000,"publicationDate":"2019-01-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":"0","resultStr":null,"platform":"Semanticscholar","paperid":null,"PeriodicalName":"Integrative cancer science and therapeutics","FirstCategoryId":"1085","ListUrlMain":"https://doi.org/10.15761/icst.1000307","RegionNum":0,"RegionCategory":null,"ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":null,"EPubDate":"","PubModel":"","JCR":"","JCRName":"","Score":null,"Total":0}
引用次数: 0
Abstract
Presence of teeth or tooth like masses at unusual sites of perioral structures like maxillary sinus, nasal cavity, ear, lip etc have been occasionally reported. But presence of fully developed dental structures with supporting skeletal tissue at non tooth bearing areas is extremely rare entity. In this report a similar case of presence of supplemental dental tissue along with supporting skeletal structure at buccal mucosa affecting facial symmetry which was associated with suspected Goldenhar Syndrome is presented. Report of such condition is extremely scanty in available literature and has been termed as OdotogenicChoriostoma by certain authors. *Correspondence to: Manjunatha BS, Associate Professor, Department of Oral Biology, Chairman, Scientific Presentation Committee, Member, Examination Unit, Faculty of Dentistry, Taif University, Kingdom of Saudi Arabia, E-mail: drmanju26@hotmail.com Received: April 09, 2019; Accepted: April 25, 2019; Published: April 29, 2019 Background Presence of tooth or tooth like structures at extragingival sites is not uncommon. Various extra gingival sites are reported for presence of such kind of structures like nasal cavity, maxillary sinus, ear, tongue as well as mandibular condylar and coronoid process. Presence of such structures may cause malocclusion, difficulty in breathing, incomplete articulation and speech alteration. Some of them are diagnosed early whereas some remain subclinical and diagnosed incidentally on radiograph. Confirmatory diagnosis for such structures is made by co relating clinical, radiographic and histological examination. Presence of tooth like structures at unusual site is considered ectopic and their presence in soft tissue is seldom observed. The term ‘‘choriostoma’’ has been proposed for such kind of structures which are histologically normal for a part of body except at the site where it is located [1]. Primary classification of choriostoma has been proposed based on its clinical and histomorphologic features like salivary gland choriostoma, osseous and cartilaginous choriostoma, glial and gastric choriostoma etc [2]. Osseous and cartilageous types of choriostoma are most commonly seen in oral cavity [1]. For presentation of such lesions with dental component as well as its location on extra gingival site, term ‘odontogenic choriostoma’ seems to be appropriate. We present an unusual case of an 8 year old girl with presence of tooth like structures in right buccal mucosa with supporting bony extension from right maxillary posterior region associated with suspected case of Goldenhar syndrome, for which term odontogenic choriostoma is used.