Bilateral Recurrent Laryngeal Nerve Palsy following Total Thyroidectomy in Triple A Syndrome, an Unexpected but Critical Complication.

IF 0.4 Q4 OTORHINOLARYNGOLOGY
Case Reports in Otolaryngology Pub Date : 2021-11-19 eCollection Date: 2021-01-01 DOI:10.1155/2021/1315117
Mathieu Chamberland, Marc-Antoine Poulin, Danielle Beaudoin
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引用次数: 0

Abstract

Introduction: Triple "A" syndrome (TAS) is a rare autosomal recessive disorder that presents in childhood with achalasia cardia, alacrima, ACTH-resistant adrenal insufficiency, with sensorimotor and autonomic polyneuropathy developing later in the course of the disease. Case Presentation. An adult white male affected by this syndrome underwent an uneventful total thyroidectomy for malignancy and suffered delayed bilateral recurrent laryngeal nerve palsy in the early postoperative hours. The palsy spontaneously resolved after a five-week course.

Conclusion: Given the rarity of this severe condition and the absence of surgical or medical causes identifiable, there is possibility that it is the neurological involvement caused by TAS that predisposed the patient to this adverse outcome, precipitated by standard manipulations during surgery.

全甲状腺切除术后双侧喉返神经麻痹的三重A综合征,一个意想不到的但关键的并发症。
简介:三“A”综合征(TAS)是一种罕见的常染色体隐性遗传病,儿童期表现为贲门失弛缓症、肺水肿、acth抵抗性肾上腺功能不全,在病程后期出现感觉运动和自主神经病变。案例演示。一个成年白人男性受此综合征的影响,接受了良性甲状腺全切除术,术后早期遭受延迟性双侧喉返神经麻痹。经过五周的治疗,麻痹自行消退。结论:鉴于这种严重疾病的罕见性和缺乏可识别的外科或医学原因,有可能是由TAS引起的神经系统受累使患者易患这种不良结果,并在手术期间通过标准操作引起。
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来源期刊
Case Reports in Otolaryngology
Case Reports in Otolaryngology OTORHINOLARYNGOLOGY-
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审稿时长
13 weeks
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