Left pulmonary aplasia with ipsilateral renal agenesis and double superior vena cava in a term neonate: a case report.

IF 0.6 Q3 MEDICINE, GENERAL & INTERNAL

Oxford Medical Case Reports Pub Date : 2026-10-09 eCollection Date: 2026-10-01 DOI:10.1093/omcr/omag192

Janaa Issa, Ahmad Fasfoos, Nardeen Hroub, Doaa Alqam, Ahmad Shalaldeh, Ammar Yousef Hmidat

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引用次数: 0

Abstract

Background: Unilateral pulmonary agenesis/aplasia is rare and often accompanied by extrapulmonary anomalies that affect prognosis.

Case report: A term male neonate delivered by cesarean section for fetal distress required brief invasive ventilation and was subsequently stabilized. Chest radiography revealed left hemithorax opacification. Contrast-enhanced CT on day 4 demonstrated a reduced left hemithorax with an absent left pulmonary parenchyma, a blind-ending left main bronchus, and an absent ipsilateral pulmonary arterial supply, consistent with left pulmonary aplasia. Evaluation also identified left renal agenesis with compensatory right renal hypertrophy and double superior vena cava, with discordant drainage descriptions across modalities requiring confirmation. The infant transitioned to room air, established feeds, and was discharged clinically stable on day 9 after birth.

Conclusion: Definitive anatomic characterization of unilateral thoracic opacity in neonates should prompt systematic cardiovascular and genitourinary screening and coordinated multidisciplinary follow-up in an outpatient setting.

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左肺发育不全合并同侧肾发育不全及双上腔静脉1例。

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来源期刊

Oxford Medical Case Reports MEDICINE, GENERAL & INTERNAL-

CiteScore

0.90

自引率

0.00%

发文量

125

审稿时长

19 weeks

期刊介绍： Oxford Medical Case Reports (OMCR) is an open access, peer-reviewed online journal publishing original and educationally valuable case reports that expand the field of medicine. The journal covers all medical specialities including cardiology, rheumatology, nephrology, oncology, neurology, and reproduction, comprising a comprehensive resource for physicians in all fields and at all stages of training. Oxford Medical Case Reports deposits all articles in PubMed Central (PMC). Physicians and researchers can find your work through PubMed , helping you reach the widest possible audience. The journal is also indexed in the Web of Science Core Collection . Oxford Medical Case Reports publishes case reports under the following categories: Allergy Audiovestibular medicine Cardiology and cardiovascular systems Critical care medicine Dermatology Emergency medicine Endocrinology and metabolism Gastroenterology and hepatology Geriatrics and gerontology Haematology Immunology Infectious diseases and tropical medicine Medical disorders in pregnancy Medical ophthalmology Nephrology Neurology Oncology Paediatrics Pain Palliative medicine Pharmacology and pharmacy Psychiatry Radiology, nuclear medicine, and medical imaging Respiratory disorders Rheumatology Sexual and reproductive health Sports Medicine Substance abuse.