X-linked hypophosphatemic rickets: case report with perspectives and challenges.

IF 1.1 Q2 MEDICINE, GENERAL & INTERNAL
Einstein-Sao Paulo Pub Date : 2026-09-25 eCollection Date: 2026-01-01 DOI:10.31744/einstein_journal/2026RC1788
Beatriz Almeida Ribeiro, Henrique Massashi Soga, Fernanda Teresa de Lima, Amancio Ramalho Júnior, Cintia Giunchetti Strabelli Nascimento, Eduardo Juan Troster, Teresa Cristina Gomes Alfinito Vieira
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引用次数: 0

Abstract

X-linked dominant hypophosphatemic rickets (XLH) is a rare genetic disorder caused by mutations in the PHEX gene and characterized by chronic hypophosphatemia due to dysregulation of fibroblast growth factor 23 (FGF23). This condition leads to bone deformities, growth impairment, and chronic pain. Conventional treatment with oral phosphate and calcitriol often has limited efficacy and is associated with adverse effects such as hyperparathyroidism and nephrocalcinosis. This case report describes the therapeutic outcomes of three pediatric patients with XLH treated with burosumab, a monoclonal antibody targeting FGF23. Burosumab acts directly on the underlying pathophysiology of the disease, improving phosphate homeostasis and bone metabolism. The patients showed improvements in clinical symptoms and biochemical parameters, with fewer adverse effects and greater treatment adherence compared with traditional therapy. These findings highlight burosumab as a promising and potentially more effective alternative for managing XLH in pediatric patients.

x连锁低磷血症佝偻病:病例报告的观点和挑战。
x连锁显性低磷血症佝偻病(XLH)是一种罕见的遗传性疾病,由PHEX基因突变引起,以成纤维细胞生长因子23 (FGF23)失调引起的慢性低磷血症为特征。这种情况会导致骨骼畸形、生长障碍和慢性疼痛。口服磷酸盐和骨化三醇的常规治疗通常疗效有限,并伴有甲状旁腺功能亢进和肾钙化症等不良反应。本病例报告描述了3例儿科XLH患者使用靶向FGF23的单克隆抗体burosumab治疗的治疗结果。Burosumab直接作用于该疾病的潜在病理生理,改善磷酸盐稳态和骨代谢。与传统疗法相比,患者临床症状和生化指标均有所改善,不良反应较少,治疗依从性更强。这些发现强调了布罗单抗作为治疗儿科患者XLH的一种有希望和潜在的更有效的替代方案。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
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来源期刊
Einstein-Sao Paulo
Einstein-Sao Paulo MEDICINE, GENERAL & INTERNAL-
CiteScore
2.00
自引率
0.00%
发文量
210
审稿时长
38 weeks
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