Simultaneous Orthognathic Surgery and Costal Bone Grafting in Hemifacial Microsomia: A Rare Case Report and Literature Review.

IF 1.3 4区 医学 Q2 Dentistry
Cleft Palate-Craniofacial Journal Pub Date : 2026-11-01 Epub Date: 2026-03-03 DOI:10.1177/10556656261426396
Chi Hyun Lee, Hyun Seung Lee, Youn-Kyung Choi, Lun-Jou Lo, So Yeon Jung, Rafael Denadai, Hyung Joon Seo
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引用次数: 0

Abstract

Hemifacial microsomia (HFM) is a congenital craniofacial anomaly frequently associated with mandibular hypoplasia. Achieving stable correction in severe cases remains challenging due to abnormal mandibular anatomy and deficient temporomandibular joint structures. We report a rare revision case of a 20-year-old female with type IIA HFM who developed progressive postoperative resorption following two-jaw surgery, resulting in a "floating" ramus-condyle segment and subsequent recurrent facial asymmetry. Revision surgery consisted of unilateral sagittal split ramus osteotomy on the unaffected side, combined with long-plate fixation and costal bone grafting on the affected side. A distal portion of the harvested costal bone was trimmed and vertically split into smaller fragments and interposed as free bone grafts between the proximal and distal mandibular segments, while the main portion was applied laterally as an onlay graft. Postoperative follow-up confirmed preservation of mandibular height with an acceptable occlusion, and secondary fat grafting further refined the soft-tissue contour. This case suggests that integrating orthognathic surgery with autogenous bone grafting may provide a durable solution in complex revision scenarios. It also highlights the importance of individualized planning and combined skeletal-soft tissue approaches to achieve favorable aesthetics.

同时正颌手术及肋骨移植治疗面肌短小症一例罕见病例报告及文献复习。
半面小畸形(HFM)是一种先天性颅面畸形,通常与下颌发育不全有关。由于下颌解剖异常和颞下颌关节结构缺陷,在严重病例中实现稳定矫正仍然具有挑战性。我们报告一个罕见的翻修病例,一名20岁的女性IIA型HFM患者在双颌手术后出现进行性骨吸收,导致“漂浮”的支髁节和随后复发的面部不对称。翻修手术为未患侧单侧矢状分叉支截骨,合并患侧长钢板固定及肋骨植骨。切除的远端肋骨被修剪并垂直分裂成更小的碎片,作为游离骨移植物插入下颌近端和远端节段之间,而主要部分被横向应用作为嵌板移植物。术后随访证实下颌高度保留,咬合良好,二次脂肪移植进一步改善软组织轮廓。本病例提示,将正颌手术与自体骨移植相结合可能为复杂翻修方案提供持久的解决方案。它还强调了个性化规划和骨骼-软组织结合方法的重要性,以实现良好的美学。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
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来源期刊
Cleft Palate-Craniofacial Journal
Cleft Palate-Craniofacial Journal DENTISTRY, ORAL SURGERY & MEDICINE-SURGERY
CiteScore
2.20
自引率
36.40%
发文量
0
审稿时长
4-8 weeks
期刊介绍: The Cleft Palate-Craniofacial Journal (CPCJ) is the premiere peer-reviewed, interdisciplinary, international journal dedicated to current research on etiology, prevention, diagnosis, and treatment in all areas pertaining to craniofacial anomalies. CPCJ reports on basic science and clinical research aimed at better elucidating the pathogenesis, pathology, and optimal methods of treatment of cleft and craniofacial anomalies. The journal strives to foster communication and cooperation among professionals from all specialties.
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