Alternative treatment for refractory Jacquet dermatitis after Hirschsprung disease surgery: A case report

IF 0.2 Q4 PEDIATRICS
Sinan Kılıç , Ahmet Güven , Sakine Işık
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Abstract

Introduction

Jacquet's erosive diaper dermatitis (JDD) is a severe form of diaper dermatitis, characterized by papuloerythematous erosions with crater-like borders in the genital and perianal regions.

Case presentation

A 2-year-old male patient was diagnosed with Hirschsprung disease (HD) during the neonatal period. A transition zone was detected in the rectosigmoid region on a contrast enema. Full-thickness rectal biopsy confirmed aganglionosis, and a colostomy was created from the transverse colon. At 18 months of age, the patient underwent the Swenson procedure, and the colostomy was closed during the same session. Following the operation, spontaneous stool passage was achieved. Approximately six months after surgery, ulcerative lesions characteristic of Jacquet dermatitis developed in the perianal region. Despite six months of treatment with moisturizers, regenerative, epithelializing, and barrier therapies (e.g., zinc oxide, madecassoside, shea butter, glycerin, oatmeal, hyaluronic acid), the lesions did not improve. However, after initiating treatment with pure Aloe Vera gel, including a 10 % diluted natural extract applied four times daily, plus a dairy-free diet for three weeks, a rapid clinical response was observed, with visible improvement within the same period.

Conclusion

The combination of Aloe Vera-based ointment plus dairy-free diet seems to be an effective management strategy for children with post pull-through Jacquet's dermatitis.
巨结肠手术后难治性雅凯皮炎的替代治疗:1例报告
雅凯(jacquet)糜烂性尿布皮炎(JDD)是一种严重的尿布皮炎,其特征是生殖器和肛周区域丘疹性红斑糜烂伴火山口样边界。1例2岁男性患者在新生儿期被诊断为先天性巨结肠病(HD)。对比灌肠时,在直肠乙状结肠区发现一个过渡区。全层直肠活检证实神经节病,并从横结肠造口。在18个月大时,患者接受了Swenson手术,并在同一疗程中关闭了结肠造口。手术后,大便自然排出。手术后大约6个月,雅凯皮炎的溃疡性病变在肛周区域发展。尽管用了6个月的保湿剂、再生、上皮化和屏障疗法(如氧化锌、鹿皮苷、乳木果油、甘油、燕麦片、透明质酸)治疗,病变并没有改善。然而,在开始使用纯芦荟凝胶治疗后,包括每天使用四次10%稀释的天然提取物,加上三周的无乳制品饮食,观察到快速的临床反应,在同一时期内有明显的改善。结论芦荟软膏联合无乳饮食治疗儿童雅凯皮炎是一种有效的治疗策略。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
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来源期刊
CiteScore
0.60
自引率
25.00%
发文量
348
审稿时长
15 days
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