Alveolar Lymphangioma in Neonate: A Case Report With Immune Profile.

IF 2.3 3区 医学 Q2 DENTISTRY, ORAL SURGERY & MEDICINE
Muhammad Aiman Bin Mohd Nizar, Benedict Seo, Haizal M Hussaini, Brendan Young, Alison M Rich
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引用次数: 0

Abstract

Background: Alveolar lymphangioma is a rare condition that commonly develops on the alveolar ridge of Black male neonates. It typically presents as a bluish, dome-shaped swelling smaller than 1 cm on the posterior alveolar ridge of the mandible or/and maxilla, that allows it to be diagnosed clinically. Most previously reported cases of alveolar lymphangioma report spontaneous resolution, and biopsy is seldom performed unless the lesion becomes symptomatic or interferes with feeding.

Case report: We report a case of oral alveolar lymphangioma on the anterior maxillary alveolar ridge of an 11-day-old infant of non-black descent. The lesion presented as a pedunculated, reddish, lobular mass in the anterior maxilla. Given its atypical presentation and the potential for feeding difficulties, an excisional biopsy was performed. The diagnosis was confirmed histologically through biopsy and supported by immunohistochemical staining.

Conclusion: This case expands the understanding of alveolar lymphangioma by reporting it in a non-Black neonate with an unusual location and appearance, emphasising the need for excisional biopsy to rule out other potential oral lesions, especially neoplasms.

新生儿肺泡淋巴管瘤:一例具有免疫特征的报告。
背景:肺泡淋巴管瘤是一种罕见的疾病,通常发生在黑人男性新生儿的肺泡嵴。它通常表现为下颌骨或/和上颌骨后牙槽嵴上小于1厘米的浅蓝色圆顶状肿胀,这使得它可以在临床上诊断。大多数先前报道的肺泡淋巴管瘤病例报告自发消退,除非病变出现症状或干扰进食,否则很少进行活检。病例报告:我们报告一例口腔牙槽淋巴管瘤的前上颌牙槽嵴的11天大的婴儿非黑血统。病变表现为上颌骨前有带梗的红色小叶状肿块。鉴于其不典型的表现和潜在的喂养困难,切除活检进行。通过组织活检和免疫组织化学染色证实了诊断。结论:本病例报告了一名位置和外观异常的非黑人新生儿的肺泡淋巴管瘤,扩大了对其的认识,强调了切除活检以排除其他潜在口腔病变,特别是肿瘤的必要性。
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来源期刊
CiteScore
5.50
自引率
2.60%
发文量
82
审稿时长
6-12 weeks
期刊介绍: The International Journal of Paediatric Dentistry was formed in 1991 by the merger of the Journals of the International Association of Paediatric Dentistry and the British Society of Paediatric Dentistry and is published bi-monthly. It has true international scope and aims to promote the highest standard of education, practice and research in paediatric dentistry world-wide. International Journal of Paediatric Dentistry publishes papers on all aspects of paediatric dentistry including: growth and development, behaviour management, diagnosis, prevention, restorative treatment and issue relating to medically compromised children or those with disabilities. This peer-reviewed journal features scientific articles, reviews, case reports, clinical techniques, short communications and abstracts of current paediatric dental research. Analytical studies with a scientific novelty value are preferred to descriptive studies. Case reports illustrating unusual conditions and clinically relevant observations are acceptable but must be of sufficiently high quality to be considered for publication; particularly the illustrative material must be of the highest quality.
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