难治性pr3阳性anca相关血管炎伴嗜酸性粒细胞增多,需要抗il -5治疗:1例报告

Elizabeth Anderson, Marcia A Friedman
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引用次数: 0

摘要

本报告描述了一例非常罕见和难治性的蛋白酶-3阳性抗中性粒细胞细胞质自身抗体相关血管炎病例,该病例伴有明显的嗜酸性粒细胞增多,在最大诱导治疗中加入白细胞介素-5阻断后才获得缓解。患者是一名健康的18岁女性,表现为硬膜炎、中耳炎、体质症状、皮肤和粘膜病变、弥漫性肺泡出血,并发现难治性嗜酸性粒细胞增多症,病因不明。该病例不符合诊断肉芽肿病合并多血管炎或嗜酸性肉芽肿病合并多血管炎的分类标准。尽管使用糖皮质激素、环磷酰胺和利妥昔单抗进行诱导治疗,但在加入mepolizumab之前,她的嗜酸性粒细胞没有得到缓解或正常化,这与外周血嗜酸性粒细胞的抑制和临床缓解相对应。本病例强调了分类标准的局限性和白介素-5在多模式治疗伴嗜酸性粒细胞增多的严重血管炎中的成功。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Refractory PR3-positive ANCA-associated vasculitis with eosinophilia requiring anti-IL-5 therapy: A case report.

This report describes a highly unusual and refractory case of proteinase-3-positive antineutrophil cytoplasmic autoantibody-associated vasculitis, which was associated with marked eosinophilia and only achieved remission after interleukin-5 blockade was added to maximal induction therapy. The patient was a healthy 18-year-old woman who presented with scleritis, otitis, constitutional symptoms, skin and mucosal lesions, and diffuse alveolar haemorrhage and found to have refractory eosinophilia of unclear aetiology. The case did not meet classification criteria for a diagnosis of granulomatosis with polyangiitis or eosinophilic granulomatosis with polyangiitis. Despite induction therapy with glucocorticoids, cyclophosphamide, and rituximab, she did not achieve remission or normalisation of eosinophilia until the addition of mepolizumab, which corresponded to the suppression of peripheral blood eosinophils and clinical remission. This case highlights the limitations of classification criteria and success of interleukin-5 in a multimodal treatment of severe vasculitis with eosinophilia.

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