杜氏和贝克尔肌营养不良症的癫痫特征。

Praveen Kumar Ramani, Kindann Fawcett, Debra Guntrum, Hallie Samuel, Emma Ciafaloni, Aravindhan Veerapandiyan
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引用次数: 0

摘要

肌营养不良症涵盖了一系列x连锁肌肉疾病,包括杜氏肌营养不良症(DMD)、贝克肌营养不良症(BMD)和由DMD基因致病性变异引起的心肌病。大约三分之一的肌营养不良患者出现神经精神症状。癫痫已经被描述过了。在此,我们报告患有肌营养不良症和癫痫的男孩的癫痫发作和脑电图特征。这是对阿肯色儿童医院和罗切斯特大学医学中心的8例肌营养不良症和癫痫患者的回顾性分析。6例为DMD, 2例为BMD。5例患者有全身性癫痫。3例患者有局灶性癫痫,其中2例癫痫发作难治性。5例患者的脑成像在正常范围内。6例患者脑电图异常。在目前的抗癫痫药物治疗方案下,所有患者的癫痫发作都得到了很好的控制。需要进一步的研究来更好地阐明潜在的机制和基因型-表型相关性。
本文章由计算机程序翻译,如有差异,请以英文原文为准。

Epilepsy Characteristics in Duchenne and Becker Muscular Dystrophies.

Epilepsy Characteristics in Duchenne and Becker Muscular Dystrophies.

Epilepsy Characteristics in Duchenne and Becker Muscular Dystrophies.

Dystrophinopathies cover a spectrum of X-linked muscle disorders including Duchenne muscular dystrophy (DMD), Becker muscular dystrophy (BMD), and cardiomyopathy due to pathogenic variants in the DMD gene. Neuropsychiatric manifestations occur approximately in one-third of patients with dystrophinopathy. Epilepsy has been described. Here we report seizure and electroencephalographic features of boys with dystrophinopathy and epilepsy. This is a retrospective chart review of eight patients with dystrophinopathy and epilepsy seen at Arkansas Children's Hospital and University of Rochester Medical center. Six patients had DMD and two had BMD. Five patients had generalized epilepsy. Three patients had focal epilepsy and the seizures were intractable in two of them. Brain imaging was available for five patients and were within normal limits. EEG abnormalities were noted in six patients. Seizures were well controlled on the current antiepileptic medication regimen in all patients. Further research is needed to better elucidate the underlying mechanisms and genotype-phenotype correlations.

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