胸腺瘤有三重威胁:纯红细胞发育不全、自身免疫性溶血性贫血和t细胞大颗粒淋巴细胞白血病。

IF 1.3 Q4 HEMATOLOGY
Tara Seibert, Patrick J Loehrer, Andrew R W O'Brien
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引用次数: 0

摘要

胸腺瘤是一种罕见的前纵隔肿瘤,常伴有副肿瘤综合征。虽然重症肌无力是最常见和众所周知的,但报道的胸腺瘤伴随的副肿瘤综合征的清单是广泛的和不断增长的。副肿瘤综合征可涉及几乎所有器官系统,包括影响任何或所有细胞系的血液学异常。这对临床医生在诊断、预后影响和管理方面提出了挑战。我们报告一位先前健康的41岁女性,被诊断患有胸腺瘤和三种罕见的血液副肿瘤综合征:纯红细胞发育不全(PRCA)、自身免疫性溶血性贫血(AIHA)和t细胞大颗粒淋巴细胞白血病(T-LGLL)。据我们所知,在同一例胸腺瘤患者中,只有另外4例报道了PRCA和AIHA,所有这些病例都接受了胸腺切除术的治疗。在本病例中,术前手术切除是不可能的,因此患者接受了皮质类固醇和奥曲肽的替代治疗,这证明了贫血的成功解决。作者提出这个病例是为了分享胸腺瘤相关的PRCA和AIHA的替代治疗策略的发现,并强调对这些复杂患者进行常规血液检查时仔细监测的重要性。
本文章由计算机程序翻译,如有差异,请以英文原文为准。

Thymoma With Triple Threat: Pure Red Cell Aplasia, Autoimmune Hemolytic Anemia, and T-Cell Large Granular Lymphocytic Leukemia.

Thymoma With Triple Threat: Pure Red Cell Aplasia, Autoimmune Hemolytic Anemia, and T-Cell Large Granular Lymphocytic Leukemia.

Thymoma With Triple Threat: Pure Red Cell Aplasia, Autoimmune Hemolytic Anemia, and T-Cell Large Granular Lymphocytic Leukemia.

Thymoma With Triple Threat: Pure Red Cell Aplasia, Autoimmune Hemolytic Anemia, and T-Cell Large Granular Lymphocytic Leukemia.

Thymomas are a rare neoplasm of the anterior mediastinum and often associated with paraneoplastic syndromes. Though myasthenia gravis is the most common and well-known, the list of reported paraneoplastic syndromes occurring with thymoma is extensive and ever-growing. Paraneoplastic syndromes can involve nearly every organ system, including hematologic abnormalities affecting any or all cell lines. This can present challenges to the clinician in terms of diagnosis, prognostic impact, and management. We present the case of a previously healthy 41-year-old female who was diagnosed with thymoma and three rare hematologic paraneoplastic syndromes: pure red cell aplasia (PRCA), autoimmune hemolytic anemia (AIHA), and T-cell large granular lymphocytic leukemia (T-LGLL). To the best of our knowledge, there have been only four other reported cases of PRCA and AIHA in a single patient with thymoma, all of which were treated with thymectomy. Upfront surgical resection was not possible in the present case and thus the patient was alternatively treated with corticosteroids and octreotide, which proved successful in resolving the anemia. The authors present this case to share these findings of an alternative treatment strategy for thymoma-associated PRCA and AIHA and to highlight the importance of careful monitoring with routine blood work for these complex patients.

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Journal of hematology
Journal of hematology HEMATOLOGY-
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