炎症性肠病患者的医源性免疫缺陷相关淋巴细胞增生性疾病。

Journal of Medical Cases Pub Date : 2022-10-01 Epub Date: 2022-10-31 DOI:10.14740/jmc3798
Benjamin D German, Jennifer Akin, Seo-Hyun Kim, Caitlin Murphy, Parameswaran Venugopal, Nicolas Lopez-Hisijos, Deborah A Katz
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引用次数: 0

摘要

原发性结直肠淋巴瘤非常罕见,而孤立于结直肠区域的医源性免疫缺陷相关淋巴细胞增生性疾病(IILPD)更是罕见。免疫缺陷相关的淋巴细胞增生性疾病可与原发性免疫疾病如炎症性肠病(IBDs)相关,通常用各种免疫调节药物治疗。在免疫调节药物中,特别是硫嘌呤类药物,已知具有显著增加iilpd发展的相对风险。在这里,我们提出了一个病例,43岁的白人男性,22年的IBD病史,长期接受免疫调节治疗,表现为严重的直肠疼痛和引流。他在麻醉下接受了硬直肠镜检查,并在直肠乙状结肠连接处后壁的硬外生组织上进行了活检。病理检查显示为IILPD。他接受了利妥昔单抗、环磷酰胺、阿霉素、长春新碱、强的松(R-CHOP)治疗,并获得完全缓解。文献表明,使用免疫调节剂如硫唑嘌呤已被证明可显著改善IBD患者的生活质量。然而,虽然任何患者发生淋巴瘤的绝对风险仍然很低,但积极使用硫嘌呤治疗的患者发生淋巴瘤的相对风险是中等的。因此,决定继续使用硫嘌呤治疗,特别是在长期治疗的情况下,需要广泛讨论并对患者进行风险/益处教育,同时密切监测新的或非特征性症状。
本文章由计算机程序翻译,如有差异,请以英文原文为准。

Iatrogenic Immunodeficiency Associated Lymphoproliferative Disorder in a Patient With Inflammatory Bowel Disease.

Iatrogenic Immunodeficiency Associated Lymphoproliferative Disorder in a Patient With Inflammatory Bowel Disease.

Iatrogenic Immunodeficiency Associated Lymphoproliferative Disorder in a Patient With Inflammatory Bowel Disease.

Primary colorectal lymphoma is incredibly rare and cases of iatrogenic immunodeficiency associated lymphoproliferative disorder (IILPD) isolated to colorectal area are even more uncommon. Immunodeficiency associated lymphoproliferative disorders can occur in association with primary immune disorders such as inflammatory bowel diseases (IBDs) which are often treated with various immunomodulatory drugs. Of the immunomodulatory drugs, thiopurines, in particular, are known to have a significantly increased relative risk for development of IILPDs. Here we present the case of a 43-year-old Caucasian man with a 22-year history of IBD treated with longstanding immunomodulatory therapy who presented with severe rectal pain and drainage. He underwent an examination under anesthesia with rigid proctoscopy and biopsies were taken of a hard exophytic appearing tissue along the posterior wall of the rectosigmoid junction. Pathological investigation of the samples revealed IILPD. He underwent treatment with rituximab, cyclophosphamide, doxorubicin, vincristine, prednisone (R-CHOP) and achieved complete remission. Literature demonstrates that the use of immunomodulators such as azathioprine has been shown to significantly improve the quality of life in patients with IBD. However, while the absolute risk of lymphoma for any given patient remains quite low, the relative risk of lymphoma in patients who are actively treated with thiopurines is moderate. Therefore, the decision to proceed with thiopurine treatment, especially in the setting of long-term therapy, requires extensive discussion and patient education of the risks/benefits along with closer monitoring of new or uncharacteristic symptoms.

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