脊髓小脑性共济失调(SCA)病例在印度的分子谱、家庭筛查和遗传咨询。

IF 1.8 4区 医学 Q3 GENETICS & HEREDITY
Journal of neurogenetics Pub Date : 2021-09-01 Epub Date: 2021-06-23 DOI:10.1080/01677063.2021.1940172
Priyanka Vishwakarma, Sarita Agarwal, Deepika Delsa Dean, Srinivasan Muthuswamy, Kausik Mandal
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引用次数: 0

摘要

脊髓小脑性共济失调(SCA)是一种成人发病的异质性疾病,具有常染色体显性遗传模式,主要由三联体重复扩增引起。SCA的临床诊断是基于表型特征,然后通过分子诊断进行确认。为了确定印度SCA病例中重复范围的状况并提供扩展的家庭筛查,我们招募了70名临床SCA疑似病例。在分子诊断方面,采用多重PCR (M-PCR)对印度常见SCA亚型1、2、3、6、7、10、12和17进行检测。在SCA2, 7和10中进一步使用TP-PCR来识别更大的扩增。70例疑似SCA患者中有18例(25%)对各种SCA亚型呈阳性(5例SCA1(28%), 6例SAC2(34%), 2例SCA3(12%), 3例SCA7 (16%), SCA6(1%)和SCA17(1%)亚型各1例)。向所有阳性病例提供了遗传咨询和大家庭筛查,并发现了另外9例病例。我们建立了M-PCR和TP-PCR检测SCA疑似病例CAG重复扩增。该方法可以可靠、快速、经济地确定SCA亚型。sca相关基因的遗传表征具有重要的临床意义,可以为临床医生和家属提供更多的预后信息和指导。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Molecular spectrum, family screening and genetic counselling of Spinocerebellar Ataxia (SCA) cases in an Indian scenario.

Spinocerebellar Ataxia (SCA) is a heterogeneous adult-onset disorder with an autosomal dominant inheritance pattern mainly caused by triplet repeat expansions. Clinical diagnosis of SCA is based on phenotypic features followed by confirmation through molecular diagnosis. To identify status of repeat range in Indian SCA cases and provide extended family screening, we enrolled 70 clinical SCA suspects. For molecular diagnosis, multiplex PCR (M-PCR) was used for common Indian SCA subtypes 1, 2, 3, 6, 7, 10, 12 and 17. TP-PCR was further used in SCA2, 7 and 10 to identify larger expansions. Eighteen out of 70 SCA suspects (25%) were found to be positive for various SCA subtypes- (5 SCA1 (28%), 6 SAC2 (34%), 2 SCA3 (12%), 3 SCA7 (16%) and one each for SCA6 (1%) and SCA17 (1%) subtypes). Genetic counselling and extended family screening were offered to all positive cases and yielded additional nine cases. We have established M-PCR and TP-PCR to detect the CAG repeat expansion in SCA suspects. This method can confirm SCA subtypes in a reliable, rapid and cost-effective way. Genetic characterization of SCA-related genes has great clinical relevance, as it could provide additional information and guidance to clinicians and family members regarding prognosis.

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来源期刊
Journal of neurogenetics
Journal of neurogenetics 医学-神经科学
CiteScore
4.40
自引率
0.00%
发文量
13
审稿时长
>12 weeks
期刊介绍: The Journal is appropriate for papers on behavioral, biochemical, or cellular aspects of neural function, plasticity, aging or disease. In addition to analyses in the traditional genetic-model organisms, C. elegans, Drosophila, mouse and the zebrafish, the Journal encourages submission of neurogenetic investigations performed in organisms not easily amenable to experimental genetics. Such investigations might, for instance, describe behavioral differences deriving from genetic variation within a species, or report human disease studies that provide exceptional insights into biological mechanisms
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