Lilia Oreto, Gian Luca Vita, Giuseppe Mandraffino, Scipione Carerj, Maria Pia Calabrò, Roberta Manganaro, Maurizio Cusmà-Piccione, Maria Chiara Todaro, Maria Sframeli, Maria Cinquegrani, Antonio Toscano, Giuseppe Vita, Sonia Messina, Concetta Zito
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According to the median age, patients were then divided into younger and older than 9 years, and compared to 24 age-matched healthy subjects. Six-minute-walk test (6MWT), North Star Ambulatory Assessment (NSAA), and a comprehensive cardiac evaluation were performed. Although EF was within the normal range, DMD patients had significantly lower values than healthy controls, and the same occurred for the remaining conventional systolic and diastolic indices. Global longitudinal strain (GLS) was reduced in all patients (older and younger, both p < 0.001). Global circumferential strain (GCS) was reduced only in older patients (< 0.001). Both GLS and GCS worsened with age in DMD patients (GLS p = 0.005; GCS p = 0.024). GLS was significantly worse in the apical segments and in the postero-lateral wall. GCS in the antero-septal, anterior and antero-lateral segments was significantly reduced in older patients, with a prevalent involvement of the sole septal wall in the younger boys. 6MWT appeared to be correlated inversely to GLS and directly to EF. A longitudinal evaluation should be scheduled in DMD boys to assess the global cardiac performance over time and to evaluate the impact of therapies.</p>","PeriodicalId":35953,"journal":{"name":"Acta Myologica","volume":"39 4","pages":"191-199"},"PeriodicalIF":0.0000,"publicationDate":"2020-12-01","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"https://ftp.ncbi.nlm.nih.gov/pub/pmc/oa_pdf/b3/34/am-2020-04-191.PMC7783425.pdf","citationCount":"8","resultStr":"{\"title\":\"Impaired myocardial strain in early stage of Duchenne muscular dystrophy: its relation with age and motor performance.\",\"authors\":\"Lilia Oreto, Gian Luca Vita, Giuseppe Mandraffino, Scipione Carerj, Maria Pia Calabrò, Roberta Manganaro, Maurizio Cusmà-Piccione, Maria Chiara Todaro, Maria Sframeli, Maria Cinquegrani, Antonio Toscano, Giuseppe Vita, Sonia Messina, Concetta Zito\",\"doi\":\"10.36185/2532-1900-022\",\"DOIUrl\":null,\"url\":null,\"abstract\":\"<p><p>Duchenne muscular dystrophy (DMD) is complicated by an early and progressive left ventricular (LV) dysfunction. 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引用次数: 8
摘要
杜氏肌营养不良症(DMD)并发早期和进行性左心室(LV)功能障碍。尽管射血分数(EF)的降低通常出现在第二个十年,但左室力学的细微变化可以更早地被发现。通过斑点跟踪超声心动图(STE)评估纵向和周向左室变形,被认为是早期功能障碍的敏感标志。我们回顾性分析了32例左室功能保留的DMD患儿的临床和超声心动图资料。根据中位年龄,将患者分为9岁以下和9岁以上两组,并与24名年龄匹配的健康受试者进行比较。进行6分钟步行试验(6MWT)、北极星动态评估(NSAA)和心脏综合评估。虽然EF在正常范围内,但DMD患者的EF值明显低于健康对照组,其他常规收缩和舒张指数也是如此。所有患者(老年人和年轻人,均p < 0.001)的总体纵向应变(GLS)均降低。全周应变(GCS)仅在老年患者中降低(< 0.001)。DMD患者GLS和GCS均随着年龄的增长而恶化(GLS p = 0.005;GCS p = 0.024)。GLS在根尖节段和后侧壁明显较差。中隔前段、前段和前外侧段的GCS在老年患者中显著减少,在年轻男孩中普遍累及脚底中隔壁。6MWT与GLS呈负相关,与EF呈正相关。应安排对DMD男孩进行纵向评估,以评估长期以来的整体心脏表现,并评估治疗的影响。
Impaired myocardial strain in early stage of Duchenne muscular dystrophy: its relation with age and motor performance.
Duchenne muscular dystrophy (DMD) is complicated by an early and progressive left ventricular (LV) dysfunction. Despite the reduction of ejection fraction (EF) usually manifests in the second decade, subtle alterations in LV mechanics can be detected earlier. Longitudinal and circumferential LV deformation, evaluated by speckle tracking echocardiography (STE), are considered sensitive markers of early dysfunction. We retrospectively examined clinical and echocardiographic data of 32 DMD children with preserved LV function. According to the median age, patients were then divided into younger and older than 9 years, and compared to 24 age-matched healthy subjects. Six-minute-walk test (6MWT), North Star Ambulatory Assessment (NSAA), and a comprehensive cardiac evaluation were performed. Although EF was within the normal range, DMD patients had significantly lower values than healthy controls, and the same occurred for the remaining conventional systolic and diastolic indices. Global longitudinal strain (GLS) was reduced in all patients (older and younger, both p < 0.001). Global circumferential strain (GCS) was reduced only in older patients (< 0.001). Both GLS and GCS worsened with age in DMD patients (GLS p = 0.005; GCS p = 0.024). GLS was significantly worse in the apical segments and in the postero-lateral wall. GCS in the antero-septal, anterior and antero-lateral segments was significantly reduced in older patients, with a prevalent involvement of the sole septal wall in the younger boys. 6MWT appeared to be correlated inversely to GLS and directly to EF. A longitudinal evaluation should be scheduled in DMD boys to assess the global cardiac performance over time and to evaluate the impact of therapies.