一个希腊家庭vcp蛋白病的多方面临床表现。

Q3 Medicine
Acta Myologica Pub Date : 2017-12-01
George K Papadimas, George P Paraskevas, Thomas Zambelis, Chrisostomos Karagiaouris, Mara Bourbouli, Anastasia Bougea, Maggie C Walter, Nicolas U Schumacher, Sabine Krause, Elisabeth Kapaki
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引用次数: 0

摘要

vcp蛋白病是一种由含缬草苷蛋白突变引起的多系统神经退行性疾病。在这里,我们报告了首例希腊vcp蛋白病病例,患者为62岁,自40多岁以来缓慢进展的肌肉无力,并在去年严重恶化。他还表现出痴呆,并伴有突出的神经精神症状,包括攻击性、冷漠、苍白和强迫症。脑MRI示额叶萎缩,肌MRI示弥漫性肌萎缩。家族史呈阳性,家族中有几位成员被诊断患有运动神经元疾病、痴呆或行为症状。VCP基因测序显示一个致病性杂合错义突变p.R159H。最后,本报告强调了家族内的变异性,拓宽了vcp蛋白病的表型谱。
本文章由计算机程序翻译,如有差异,请以英文原文为准。

The multifaceted clinical presentation of VCP-proteinopathy in a Greek family.

The multifaceted clinical presentation of VCP-proteinopathy in a Greek family.

The multifaceted clinical presentation of VCP-proteinopathy in a Greek family.

The multifaceted clinical presentation of VCP-proteinopathy in a Greek family.

VCP-proteinopathy is a multisystem neurodegenerative disorder caused by mutations in valosin containing protein. Here, we report the first Greek case of VCP-proteinopathy in a 62 year old patient with a slowly progressing muscular weakness since his mid-40s and a severe deterioration during the last year. He also manifested dementia with prominent neuropsychiatric symptoms, including aggression, apathy, palilalia and obsessions. Brain MRI revealed frontal atrophy, while muscle MRI showed diffuse muscle atrophy. Family history was positive and several members of the family had been diagnosed with motor neuron disease, dementia or behavioral symptoms. Sequencing of the VCP gene revealed a pathogenic heterozygous missense mutation p.R159H. Conclusively, the present report highlights the intrafamilial variability and broadens the phenotypic spectrum of VCP-proteinopathy.

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来源期刊
Acta Myologica
Acta Myologica Medicine-Cardiology and Cardiovascular Medicine
CiteScore
3.70
自引率
0.00%
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