对严重联合免疫缺陷的代谢和营养决定因素的新见解。

Rare diseases (Austin, Tex.) Pub Date : 2015-11-24 eCollection Date: 2015-01-01 DOI:10.1080/21675511.2015.1112479
Martha S Field, Elena Kamynina, David Watkins, David S Rosenblatt, Patrick J Stover
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引用次数: 7

摘要

最近在严重联合免疫缺陷(SCID)患者中发现了MTHFD1的人类突变。SCID是由先天代谢错误引起的T细胞和b细胞增殖和功能受损。SCID最常见的原因之一是腺苷脱氨酶(ADA)缺乏,最终会抑制DNA合成和细胞分裂。MTHFD1已被证明在细胞周期的s期转移到细胞核;这种定位对于胸苷酸(dTMP或DNA中的“T”碱基)的合成以及随后的细胞周期和细胞增殖至关重要。与SCID相关的MTHFD1突变的鉴定突出了dTMP合成在SCID病因学中的潜在重要性。
本文章由计算机程序翻译,如有差异,请以英文原文为准。

New insights into the metabolic and nutritional determinants of severe combined immunodeficiency.

New insights into the metabolic and nutritional determinants of severe combined immunodeficiency.

Human mutations in MTHFD1 have recently been identified in patients with severe combined immunodeficiency (SCID). SCID results from inborn errors of metabolism that cause impaired T- and B-cell proliferation and function. One of the most common causes of SCID is adenosine deaminase (ADA) deficiency, which ultimately inhibits DNA synthesis and cell division. MTHFD1 has been shown to translocate to the nucleus during S-phase of the cell cycle; this localization is critical for synthesis of thymidyate (dTMP or the "T" base in DNA) and subsequent progression through the cell cycle and cell proliferation. Identification of MTHFD1 mutations that are associated with SCID highlights the potential importance of adequate dTMP synthesis in the etiology of SCID.

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