神经性和躯体性MPSIIIA的基因治疗。

Rare diseases (Austin, Tex.) Pub Date : 2013-12-12 eCollection Date: 2013-01-01 DOI:10.4161/rdis.27209
Virginia Haurigot, Fatima Bosch
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引用次数: 8

摘要

粘多糖病IIIA型(MPSIIIA)代表未满足的医疗需求。MPSIIIA与许多其他溶酶体贮积性疾病(LSD)具有严重的神经退行性疾病伴轻度躯体累及的特征。因此,开发新疗法的主要靶器官是中枢神经系统(CNS),但同时矫正外周疾病将大大提高整体临床疗效。我们最近开发了一种基于将血清型9腺相关病毒(AAV9)衍生载体递送至脑脊液的新型MPSIIIA治疗方法。这种基因治疗策略通过中枢神经系统、周围神经系统(PNS)和肝脏的广泛转导,在动物模型中纠正了中枢神经系统和躯体病理。这项工作为治疗人类MPSIIIA的方法的临床转化奠定了基础。在这里,我们讨论了一些重要的考虑因素,进一步支持这种治疗对MPSIIIA和其他与中枢神经系统和躯体有关的LSD的适用性。
本文章由计算机程序翻译,如有差异,请以英文原文为准。

Toward a gene therapy for neurological and somatic MPSIIIA.

Toward a gene therapy for neurological and somatic MPSIIIA.

Mucopolysaccharidosis Type IIIA (MPSIIIA) represents an unmet medical need. MPSIIIA shares with many other lysosomal storage disorders (LSD) the characteristic of being a severe neurodegenerative disease accompanied by mild somatic involvement. Thus, the main target organ for the development of new treatments is the central nervous system (CNS), but overall clinical efficacy would be greatly enhanced by simultaneous correction of peripheral disease. We have recently developed a novel treatment for MPSIIIA based on the delivery to the cerebrospinal fluid of serotype 9 adeno-associated virus (AAV9)-derived vectors. This gene therapy strategy corrected both CNS and somatic pathology in animal models through widespread transduction of CNS, peripheral nervous system (PNS), and liver. The work set the grounds for the clinical translation of the approach to treat MPSIIIA in humans. Here we discuss some important considerations that further support the applicability of this treatment to MPSIIIA and other LSD with CNS and somatic involvement.

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