携带delta F508突变的CFTR功能障碍。

Journal of cell science. Supplement Pub Date : 1993-01-01
M J Welsh, G M Denning, L S Ostedgaard, M P Anderson
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引用次数: 0

摘要

囊性纤维化跨膜传导调节因子(CFTR)在囊性纤维化(CF)患者中发生突变。最常见的cf相关突变是在CFTR δ F508残基上缺失苯丙氨酸。当在异源细胞中表达时,携带delta F508突变的CFTR不能通过正常的生物合成途径进行,不能运输到质膜。结果,CFTR δ F508定位错误,不存在于气道上皮原代培养的顶膜中。因此,CF气道上皮的顶膜是Cl-不渗透的,这一缺陷可能与疾病的发病机制有关。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Dysfunction of CFTR bearing the delta F508 mutation.

The cystic fibrosis transmembrane conductance regulator (CFTR) is mutated in patients with cystic fibrosis (CF). The most common CF-associated mutation is deletion of phenylalanine at residue 508, CFTR delta F508. When expressed in heterologous cells, CFTR bearing the delta F508 mutation fails to progress through the normal biosynthetic pathway and fails to traffic to the plasma membrane. As a result, CFTR delta F508 is mislocalized and is not present in the apical membrane of primary cultures of airway epithelia. Consequently, the apical membrane of CF airway epithelia is Cl- -impermeable, a defect that probably contributes to the pathogenesis of the disease.

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