原发性骨表现的低级别b细胞淋巴瘤的病理、临床特征和自然史。

IF 4.2 1区 医学 Q1 PATHOLOGY
Shenon Sethi, Irem Isgor, Pallavi K Galera, Efrat Luttwak, Heiko Schöder, Gilles A Salles, Ahmet Dogan
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引用次数: 0

摘要

原发性骨淋巴瘤是罕见的,大多数报道的病例为弥漫性大b细胞淋巴瘤。以原发性骨受累为表现的低级别b细胞淋巴瘤(PB-LGBCLs)远不常见,其临床病理特征和临床病程仍不明确。我们回顾性分析了在单一三级癌症中心诊断的32例pb - lgbcl。当疾病表现为仅骨骼受累,伴或不伴连续软组织延伸,在初始诊断时无淋巴结、脾脏或不连续结外疾病时,病例被纳入。记录分期、骨髓和低水平外周血受累,但不作为排除标准。该队列包括滤泡性淋巴瘤(FL; 22/ 32,69%)、边缘带淋巴瘤(MZL; 6/ 32,19%)、淋巴浆细胞性淋巴瘤(LPL; 2/ 32,6%)和慢性淋巴细胞性白血病/小淋巴细胞性淋巴瘤(CLL/SLL; 2/ 32,6%)。中位年龄为64岁(范围:39至87岁),25/32例患者(78%)患有多灶性骨骼疾病,最常累及骨盆和脊柱。原发性骨FL经常表现出传统FL的典型特征,包括生发中心b细胞表型,频繁的BCL2重排和复发性FL相关突变。非fl亚型的临床病理特征和分子表现与它们的系统性对应型一致。在27例随访超过6个月的患者中,12例患者出现疾病进展或转化。3例原发性淋巴瘤转化为弥漫性大b细胞淋巴瘤。没有人员死亡。pb - lgbcl是罕见的,FL是最常见的亚型,表现出异质性的生物学和临床行为。识别这种表现对于避免误诊为侵袭性淋巴瘤、非血淋巴性骨肿瘤或反应性疾病是很重要的。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Pathology, Clinical Features, and Natural History of Low-Grade B-Cell Lymphomas With Primary Osseous Presentation.

Primary bone lymphomas are rare, and most reported cases represent diffuse large B-cell lymphoma. Low-grade B-cell lymphomas presenting with primary osseous involvement (PB-LGBCLs) are far less common, and their clinicopathologic features and clinical course remain poorly defined. We retrospectively analyzed 32 PB-LGBCLs diagnosed at a single tertiary cancer center. Cases were included when the disease presented with bone-only involvement, with or without contiguous soft tissue extension, and without lymph node, spleen, or noncontiguous extranodal disease at initial diagnosis. Staging marrow and low-level peripheral blood involvement were recorded but were not used as exclusion criteria. The cohort included follicular lymphoma (FL; 22/32, 69%), marginal zone lymphoma (MZL; 6/32, 19%), lymphoplasmacytic lymphoma (LPL; 2/32, 6%), and chronic lymphocytic leukemia/small lymphocytic lymphoma (CLL/SLL; 2/32, 6%). Median age was 64 years (range: 39 to 87), and 25/32 patients (78%) had multifocal skeletal disease, most often involving the pelvis and spine. Primary bone FL frequently showed features typical of conventional FL, including germinal center B-cell phenotype, frequent BCL2 rearrangement, and recurrent FL-associated mutations. Non-FL subtypes showed clinicopathologic features and molecular findings compatible with their systemic counterparts. Among 27 patients with more than 6 months of follow-up, disease progression or transformation occurred in 12 patients. Three FLs transformed to diffuse large B-cell lymphoma. No deaths occurred. PB-LGBCLs are rare with FL as the most common subtype and show heterogeneous biology and clinical behavior. Recognition of this presentation is important to avoid misclassification as aggressive lymphoma, nonhematolymphoid bone neoplasm, or reactive condition.

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来源期刊
CiteScore
10.30
自引率
5.40%
发文量
295
审稿时长
1 months
期刊介绍: The American Journal of Surgical Pathology has achieved worldwide recognition for its outstanding coverage of the state of the art in human surgical pathology. In each monthly issue, experts present original articles, review articles, detailed case reports, and special features, enhanced by superb illustrations. Coverage encompasses technical methods, diagnostic aids, and frozen-section diagnosis, in addition to detailed pathologic studies of a wide range of disease entities. Official Journal of The Arthur Purdy Stout Society of Surgical Pathologists and The Gastrointestinal Pathology Society.
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