[肉碱缺乏:一种可治疗的心肌病]。

Journal of cardiography Pub Date : 1986-03-01
K Hirata, F Yoshioka, Y Eto, K Suzuki, K Yokochi, H Kato, K Ohta, M Terasawa
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引用次数: 0

摘要

这是一个报告两兄弟,6岁和5岁,系统性肉碱缺乏和心肌病,他们的症状在口服dl -肉碱后得到改善。他们从三岁起就出现了进行性肌肉无力。哥哥入院时的x线片显示心脏肥大,胸廓比例为60%,心电图显示左心室肥厚,心前导联T波高、尖峰。超声心动图显示心肌轻度增厚,射血分数降低。骨骼肌活检标本和血清评估肉碱含量。骨骼肌标本显示脂质储存性肌病,骨骼肌和血清中肉碱含量均降低。哥哥的心肌活检显示线粒体积聚。由肉碱缺乏引起的心肌病通常是致命的,但可以治愈。当遇到心脏肥大和进行性骨骼肌无力的患者时,应考虑肉碱缺乏症。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
[Carnitine deficiency: a treatable cardiomyopathy].

This is a report of two brothers, six and five years of age, with systemic carnitine deficiency and cardiomyopathy, whose symptoms were improved after oral administrations of DL-carnitine. They had had progressive muscle weakness since three years of age. The elder brother's radiograph on admission showed cardiomegaly with a cardiothoracic ratio of 60%, and his electrocardiogram showed left ventricular hypertrophy and tall, peaked T waves in the precordial leads. The echocardiogram showed slight thickening of the cardiac muscle and decreased ejection fraction. Skeletal muscle biopsy specimens and sera were assessed for carnitine content. The skeletal muscle specimens revealed lipid storage myopathy, and the carnitine contents of the skeletal muscle and sera were both decreased. Myocardial biopsy for the elder brother revealed mitochondrial accumulation. Cardiomyopathy caused by carnitine deficiency is often fatal, but may be cured. Carnitine deficiency should be considered whenever a patient with cardiomegaly and progressive skeletal muscle weakness is encountered.

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