Shan Kai Ing, Guo Ruey Ling, Yih Hoong Lee, Antony K Kuruvilla
{"title":"眼眶肌炎:硬皮病-多发性肌炎重叠综合征中一种少见的眼部表现。","authors":"Shan Kai Ing, Guo Ruey Ling, Yih Hoong Lee, Antony K Kuruvilla","doi":"10.1136/bcr-2025-267421","DOIUrl":null,"url":null,"abstract":"<p><p>Scleroderma-polymyositis overlap syndrome (SSc-PM) is an uncommon autoimmune condition characterised by clinical and serological features of both systemic sclerosis and inflammatory myopathy. Ocular manifestations of this syndrome are rare and insufficiently described in the literature. We report a case of SSc-PM presenting with orbital myositis as the primary manifestation, accompanied by proximal myopathy. A middle-aged woman presented with a 3-month history of progressive finger skin tightening, painless diplopia and restricted eye movements. Ophthalmological evaluation and imaging confirmed bilateral lateral rectus myositis. Laboratory investigations revealed elevated creatine kinase, positive antinuclear antibodies and anti-Ku antibody positivity. Following the rheumatology consultation, she was treated with intravenous methylprednisolone, transitioned to tapering oral prednisolone and initiated on mycophenolate mofetil. Her diplopia resolved completely and muscle enzyme levels normalised. Over 6 months of follow-up, there was no progression of cutaneous or pulmonary disease. This case highlights orbital myositis as a rare but treatable manifestation of SSc-PM, underscoring the importance of early recognition and prompt immunosuppression in overlap syndromes.</p>","PeriodicalId":9080,"journal":{"name":"BMJ Case Reports","volume":"18 9","pages":""},"PeriodicalIF":0.6000,"publicationDate":"2025-09-23","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"","citationCount":"0","resultStr":"{\"title\":\"Orbital myositis: an uncommon ophthalmic presentation in scleroderma-polymyositis overlap syndrome.\",\"authors\":\"Shan Kai Ing, Guo Ruey Ling, Yih Hoong Lee, Antony K Kuruvilla\",\"doi\":\"10.1136/bcr-2025-267421\",\"DOIUrl\":null,\"url\":null,\"abstract\":\"<p><p>Scleroderma-polymyositis overlap syndrome (SSc-PM) is an uncommon autoimmune condition characterised by clinical and serological features of both systemic sclerosis and inflammatory myopathy. Ocular manifestations of this syndrome are rare and insufficiently described in the literature. We report a case of SSc-PM presenting with orbital myositis as the primary manifestation, accompanied by proximal myopathy. A middle-aged woman presented with a 3-month history of progressive finger skin tightening, painless diplopia and restricted eye movements. Ophthalmological evaluation and imaging confirmed bilateral lateral rectus myositis. Laboratory investigations revealed elevated creatine kinase, positive antinuclear antibodies and anti-Ku antibody positivity. Following the rheumatology consultation, she was treated with intravenous methylprednisolone, transitioned to tapering oral prednisolone and initiated on mycophenolate mofetil. Her diplopia resolved completely and muscle enzyme levels normalised. Over 6 months of follow-up, there was no progression of cutaneous or pulmonary disease. This case highlights orbital myositis as a rare but treatable manifestation of SSc-PM, underscoring the importance of early recognition and prompt immunosuppression in overlap syndromes.</p>\",\"PeriodicalId\":9080,\"journal\":{\"name\":\"BMJ Case Reports\",\"volume\":\"18 9\",\"pages\":\"\"},\"PeriodicalIF\":0.6000,\"publicationDate\":\"2025-09-23\",\"publicationTypes\":\"Journal Article\",\"fieldsOfStudy\":null,\"isOpenAccess\":false,\"openAccessPdf\":\"\",\"citationCount\":\"0\",\"resultStr\":null,\"platform\":\"Semanticscholar\",\"paperid\":null,\"PeriodicalName\":\"BMJ Case Reports\",\"FirstCategoryId\":\"1085\",\"ListUrlMain\":\"https://doi.org/10.1136/bcr-2025-267421\",\"RegionNum\":0,\"RegionCategory\":null,\"ArticlePicture\":[],\"TitleCN\":null,\"AbstractTextCN\":null,\"PMCID\":null,\"EPubDate\":\"\",\"PubModel\":\"\",\"JCR\":\"Q3\",\"JCRName\":\"MEDICINE, GENERAL & INTERNAL\",\"Score\":null,\"Total\":0}","platform":"Semanticscholar","paperid":null,"PeriodicalName":"BMJ Case Reports","FirstCategoryId":"1085","ListUrlMain":"https://doi.org/10.1136/bcr-2025-267421","RegionNum":0,"RegionCategory":null,"ArticlePicture":[],"TitleCN":null,"AbstractTextCN":null,"PMCID":null,"EPubDate":"","PubModel":"","JCR":"Q3","JCRName":"MEDICINE, GENERAL & INTERNAL","Score":null,"Total":0}
Orbital myositis: an uncommon ophthalmic presentation in scleroderma-polymyositis overlap syndrome.
Scleroderma-polymyositis overlap syndrome (SSc-PM) is an uncommon autoimmune condition characterised by clinical and serological features of both systemic sclerosis and inflammatory myopathy. Ocular manifestations of this syndrome are rare and insufficiently described in the literature. We report a case of SSc-PM presenting with orbital myositis as the primary manifestation, accompanied by proximal myopathy. A middle-aged woman presented with a 3-month history of progressive finger skin tightening, painless diplopia and restricted eye movements. Ophthalmological evaluation and imaging confirmed bilateral lateral rectus myositis. Laboratory investigations revealed elevated creatine kinase, positive antinuclear antibodies and anti-Ku antibody positivity. Following the rheumatology consultation, she was treated with intravenous methylprednisolone, transitioned to tapering oral prednisolone and initiated on mycophenolate mofetil. Her diplopia resolved completely and muscle enzyme levels normalised. Over 6 months of follow-up, there was no progression of cutaneous or pulmonary disease. This case highlights orbital myositis as a rare but treatable manifestation of SSc-PM, underscoring the importance of early recognition and prompt immunosuppression in overlap syndromes.
期刊介绍:
BMJ Case Reports is an important educational resource offering a high volume of cases in all disciplines so that healthcare professionals, researchers and others can easily find clinically important information on common and rare conditions. All articles are peer reviewed and copy edited before publication. BMJ Case Reports is not an edition or supplement of the BMJ.