眼眶肌炎:硬皮病-多发性肌炎重叠综合征中一种少见的眼部表现。

IF 0.6 Q3 MEDICINE, GENERAL & INTERNAL
Shan Kai Ing, Guo Ruey Ling, Yih Hoong Lee, Antony K Kuruvilla
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引用次数: 0

摘要

硬皮病-多发性肌炎重叠综合征(SSc-PM)是一种罕见的自身免疫性疾病,以系统性硬化症和炎性肌病的临床和血清学特征为特征。这种综合征的眼部表现是罕见的,文献中也没有充分的描述。我们报告一例SSc-PM以眶肌炎为主要表现,并伴有近端肌病。一位中年妇女,有3个月进行性手指皮肤紧致、无痛性复视和眼球运动受限的病史。眼科检查及影像学证实双侧外侧直肌炎。实验室检查显示肌酸激酶升高,抗核抗体阳性,抗ku抗体阳性。风湿病咨询后,她接受静脉注射甲基强的松龙治疗,过渡到逐渐减少口服强的松龙,并开始使用霉酚酸酯。她的复视完全消失,肌肉酶水平恢复正常。在6个月的随访中,没有皮肤或肺部疾病的进展。该病例强调了眼窝肌炎是SSc-PM的一种罕见但可治疗的表现,强调了在重叠综合征中早期识别和及时免疫抑制的重要性。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Orbital myositis: an uncommon ophthalmic presentation in scleroderma-polymyositis overlap syndrome.

Scleroderma-polymyositis overlap syndrome (SSc-PM) is an uncommon autoimmune condition characterised by clinical and serological features of both systemic sclerosis and inflammatory myopathy. Ocular manifestations of this syndrome are rare and insufficiently described in the literature. We report a case of SSc-PM presenting with orbital myositis as the primary manifestation, accompanied by proximal myopathy. A middle-aged woman presented with a 3-month history of progressive finger skin tightening, painless diplopia and restricted eye movements. Ophthalmological evaluation and imaging confirmed bilateral lateral rectus myositis. Laboratory investigations revealed elevated creatine kinase, positive antinuclear antibodies and anti-Ku antibody positivity. Following the rheumatology consultation, she was treated with intravenous methylprednisolone, transitioned to tapering oral prednisolone and initiated on mycophenolate mofetil. Her diplopia resolved completely and muscle enzyme levels normalised. Over 6 months of follow-up, there was no progression of cutaneous or pulmonary disease. This case highlights orbital myositis as a rare but treatable manifestation of SSc-PM, underscoring the importance of early recognition and prompt immunosuppression in overlap syndromes.

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来源期刊
BMJ Case Reports
BMJ Case Reports Medicine-Medicine (all)
CiteScore
1.40
自引率
0.00%
发文量
1588
期刊介绍: BMJ Case Reports is an important educational resource offering a high volume of cases in all disciplines so that healthcare professionals, researchers and others can easily find clinically important information on common and rare conditions. All articles are peer reviewed and copy edited before publication. BMJ Case Reports is not an edition or supplement of the BMJ.
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