PS19小鼠tau病理模型中SCN起搏器的昼夜节律定时和携带特性。

IF 4.2 2区 医学 Q1 NEUROSCIENCES
Nicklaus R. Halloy , Megan Formanowicz , Nguyen Nhi Lien Pham , Kari R. Hoyt , Karl Obrietan
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引用次数: 0

摘要

tau病是由微管相关蛋白tau (MAPT)错误折叠引起的一组神经退行性疾病,导致其异常积累和过度磷酸化,导致神经元功能障碍和死亡。牛头病患者还会经历行为和睡眠的昼夜节律紊乱。tau蛋白病理与昼夜节律功能障碍之间的联系尚不清楚,特别是关于视交叉上核(SCN)的作用,视交叉上核是大脑的中央昼夜节律起搏器。在这里,我们对PS19 (Prnp-huMAPT*P301S)小鼠模型的SCN进行了组织学和功能分析。PS19小鼠的SCN早在2 月龄时就积累了磷酸化的tau,并且在SCN的两个主要神经元亚群:VIPergic(核心)和AVPergic(壳)神经元中都检测到tau病理。为了评估SCN的时间和携带特性,在3至11 月龄的PS19和野生型(WT)小鼠中监测每日运动活动。与年龄匹配的WT小鼠相比,PS19小鼠的活动谱、对光/暗周期变化的再伴随率和内在昼夜节律计时特性在很大程度上没有受到影响。最后,分析来自PS19和WT小鼠的tau原纤维种子SCN外植体的昼夜节律基因表达并没有发现网络级振荡器特性的差异。综上所述,这些发现表明,SCN内的tau病理并不足以引发该tau病模型中核心昼夜节律计时机制的显著中断。此外,这些结果提出了一种可能性,即tau病中的昼夜节律中断是由SCN门控输出通路或下游时钟门控电路的功能障碍引起的,而不是SCN振荡器本身。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Circadian timing and entrainment properties of the SCN pacemaker in the PS19 mouse model of tau pathology
Tauopathies are a group of neurodegenerative disorders caused by the misfolded microtubule-associated protein tau (MAPT), leading to its abnormal accumulation and hyperphosphorylation, and resulting in neuronal dysfunction and death. Tauopathy patients also experience disruptions to circadian rhythms of behavior and sleep. The connection between tau pathology and circadian dysfunction is not well understood, especially regarding the role of the suprachiasmatic nucleus (SCN), the brain's central circadian pacemaker. Here, we conducted histological and functional analyses of the SCN in the PS19 (Prnp-huMAPT*P301S) mouse model of tauopathy. The SCN of PS19 mice had accumulation of phosphorylated tau as early as 2 months of age, and tau pathology was detected in both major neuronal subpopulations of the SCN: VIPergic (core) and AVPergic (shell) neurons. To assess SCN timing and entrainment properties, daily locomotor activity was monitored in PS19 and wild-type (WT) mice from 3 to 11 months-of-age. Activity profiles, rates of re-entrainment to changes in the light/dark cycle, and intrinsic circadian timing properties were largely unaffected in PS19 mice compared to age-matched WT mice. Finally, profiling circadian gene expression in tau fibril-seeded SCN explants from PS19 and WT mice did not reveal differences in network-level oscillator properties. Together, these findings suggest that tau pathology within the SCN is not sufficient to trigger marked disruptions of core circadian timing mechanisms in this tauopathy model. Further, these results raise the possibility that circadian disruptions in tauopathies arise from dysfunction in SCN-gated output pathways or downstream clock-gated circuits rather than the SCN oscillator itself.
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来源期刊
Experimental Neurology
Experimental Neurology 医学-神经科学
CiteScore
10.10
自引率
3.80%
发文量
258
审稿时长
42 days
期刊介绍: Experimental Neurology, a Journal of Neuroscience Research, publishes original research in neuroscience with a particular emphasis on novel findings in neural development, regeneration, plasticity and transplantation. The journal has focused on research concerning basic mechanisms underlying neurological disorders.
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