【努南综合征伴多椎体的腰骶神经根肥大1例】。

Q4 Medicine
Clinical Neurology Pub Date : 2025-08-28 Epub Date: 2025-07-24 DOI:10.5692/clinicalneurol.cn-002094
Yukako Araga, Yoshitsugu Nakamura, Kensuke Kakiuchi, Takafumi Hosokawa, Shimon Ishida, Shigeki Arawaka
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引用次数: 0

摘要

患者为61岁男性,出生后出现感音神经性听力损失,6岁左右出现多个皮肤粟粒大小的小痣。他双侧下肢疼痛;1个月后,他来到我们医院。他没有神经或皮肤症状的家族史。在神经传导研究中,双侧胫神经的f波频率降低。腰椎磁共振成像显示双侧腰骶神经根肥大。遗传分析显示,其PTPN11基因存在杂合单碱基非同义替换(c.1403C>T, p.Thr468Met)。这种替代是已知的致病变异。我们诊断该患者患有努南综合征,有多个lentigines。这种综合征是由编码SHP-2蛋白的基因变异引起的ras病,SHP-2蛋白是RAS/丝裂原活化蛋白激酶(MAPK)信号通路的一个组成部分。脊髓神经根肿大应包括ras病变作为鉴别诊断。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
[Hypertrophy of the lumbosacral nerve roots in Noonan syndrome with multiple lentigines: a case report].

The patient was a 61-year-old man in whom sensorineural hearing loss were noted after birth and the presence of multiple cutaneous millet-sized lentigines were noted after about 6-year-old. He had pain in his bilateral lower extremities; 1 month later, he visited our hospital. He had no family history of neurological or cutaneous symptoms. In nerve conduction studies, the F-wave frequencies were reduced in the bilateral tibial nerves. In lumbar spine magnetic resonance imaging, the bilateral lumbosacral nerve roots showed hypertrophy. A genetic analysis revealed that he had a heterozygous single-base non-synonymous substitution in the PTPN11 gene (c.1403C>T, p.Thr468Met). This substitution is known pathogenic variant. We diagnosed the patient with Noonan syndrome with multiple lentigines. This syndrome is a RASopathy that is caused by variants in genes encoding the SHP-2 protein, which is a component of the RAS/mitogen-activated protein kinase (MAPK) signaling pathway. RASopathies should be included as differential diagnoses for spinal nerve root enlargement.

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来源期刊
Clinical Neurology
Clinical Neurology Medicine-Neurology (clinical)
CiteScore
0.30
自引率
0.00%
发文量
147
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