多药免疫抑制治疗抗黑色素瘤分化相关基因5抗体阳性皮肌炎后的其他医源性免疫缺陷相关淋巴细胞增生性疾病1例报告

IF 0.9 Q4 RHEUMATOLOGY
Shungo Mochizuki, Toshiki Nakajima, Shota Ohsumi, Aiko Ogura, Nozomi Akatsu, Noriyoshi Takebe, Kentaro Odani, Toshiyuki Kitano, Yoshitaka Imura
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引用次数: 0

摘要

虽然其他医源性免疫缺陷相关淋巴细胞增生性疾病(olia - lpd)很少见,但它们是免疫抑制治疗的重要不良反应。尽管抗黑色素瘤分化相关基因5 (MDA5)抗体阳性的皮肌炎需要多药物免疫抑制治疗来控制间质性肺炎,但oia - lpd很少有报道。此外,中枢神经系统(CNS)的olia - lpd从未被记录。在这里,我们报告了一例中枢神经系统的olia - lpd,可能是由于治疗MDA5抗体阳性的皮肌炎引起的。一名53岁女性被诊断为MDA5皮肌炎,并使用强的松龙(PSL)、他克莫司和静脉环磷酰胺脉冲治疗的多药免疫抑制治疗快速进展间质性肺疾病。治疗开始七个月后,呕吐导致小脑肿瘤的发现。小脑肿瘤组织学上为eb病毒编码的小rna阳性弥漫性大b细胞淋巴瘤,血液中EBV- dna阳性。由于EBV再激活,患者被诊断为olia - lpd。化疗,包括高剂量甲氨蝶呤(MTX)和利妥昔单抗,预防肿瘤复发而不加剧间质性肺疾病。这是第一例报道的中枢性olia - lpd合并多药免疫抑制的MDA5皮肌炎患者。化疗,包括大剂量MTX和利妥昔单抗,可用于中枢性olia - lpd,而不会加重已解决的间质性肺疾病。在olia - lpd治疗期间,MDA5皮肌炎的活性可以用低剂量的PSL来控制。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Other iatrogenic immunodeficiency-associated lymphoproliferative disorders after multidrug immunosuppressive therapy for anti-melanoma differentiation association gene 5 antibody-positive dermatomyositis: a case report.

Although other iatrogenic immunodeficiency-associated lymphoproliferative disorders (OIIA-LPDs) are rare, they are important adverse effects of immunosuppressive therapies. Even though anti-melanoma differentiation association gene 5 (MDA5) antibody-positive dermatomyositis requires multidrug immunosuppressive therapy for interstitial pneumonia control, OIIA-LPD has rarely been reported. Moreover, central nervous system (CNS) OIIA-LPD has never been documented. Here, we report a case of CNS OIIA-LPD that may have been caused by treatment for MDA5 antibody-positive dermatomyositis. A 53-year-old woman was diagnosed with MDA5 dermatomyositis and treated for rapidly progressive interstitial lung disease using multidrug immunosuppressive therapy with prednisolone (PSL), tacrolimus, and intravenous cyclophosphamide pulse therapy. Seven months after treatment initiation, vomiting led to the discovery of a cerebellar tumour. The cerebellar tumour was histologically Epstein-Barr virus (EBV)-encoded small RNA-positive diffuse large B-cell lymphoma, with EBV-DNA being positive in the blood. The patient was diagnosed with OIIA-LPDs due to EBV reactivation. Chemotherapy, including high-dose methotrexate (MTX) and rituximab, prevented tumour recurrence without exacerbating interstitial lung disease. This is the first reported case of CNS OIIA-LPD with multidrug immunosuppression in a patient with MDA5 dermatomyositis. Chemotherapy, including high-dose MTX and rituximab, can be used for central OIIA-LPD without aggravating settled interstitial lung disease. The activity of MDA5 dermatomyositis during OIIA-LPD treatment may be managed with low-dose PSL.

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