利用全转录组和空间转录组方法对颅咽管瘤进行综合分子表征。

IF 2.7 3区 医学 Q2 CLINICAL NEUROLOGY
Špela Kert, Alenka Matjašič, Jože Pižem, Jernej Mlakar, Matic Bošnjak, Miha Jerala, Primož Kotnik, Barbara Faganel Kotnik, Lidija Kitanovski, Andrej Zupan
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引用次数: 0

摘要

颅咽管瘤(Craniopharyngiomas, CPs)是一种罕见的良性脑肿瘤,WHO将其分类为I级,分为两种亚型:金刚瘤性颅咽管瘤(adantinomous颅咽管瘤,ACP)和乳头状颅咽管瘤(papillary craniopharyngioma, PCP)。ACP是由激活Wnt信号通路的CTNNB1基因外显子3的体细胞突变引起的。PCP与体细胞BRAF p.V600E突变激活MAPK信号通路有关。了解它们的分子差异对诊断和治疗至关重要。本研究旨在利用大量转录组测序和原位空间转录组学分析ACP和PCP常见的体细胞改变。采用RNA测序和高分辨率空间谱检测突变,并检测ACP、PCP和健康垂体组织之间的基因表达差异。对24个肿瘤样本进行全转录组测序,并从GTEx门户获取健康垂体数据。生物信息学分析利用CTAT突变管道,用Sanger测序进行验证。结果证实BRAF p.V600E突变存在于所有PCP样本中,CTNNB1突变存在于所有ACP样本中。差异基因表达分析强调了不同的分子谱,并强化了Wnt和MAPK信号的参与。空间分析鉴定了41个ACP和PCP之间的差异表达基因。这项研究为CP生物学提供了重要的见解,支持改进诊断和潜在的治疗策略。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Comprehensive molecular characterization of craniopharyngiomas using whole transcriptome and spatial transcriptomics approaches.

Craniopharyngiomas (CPs) are rare benign brain tumors that are classified as WHO grade I, with two subtypes: adamantinomatous craniopharyngioma (ACP) and papillary craniopharyngioma (PCP). ACP is caused by somatic mutations in exon 3 of the CTNNB1 gene activating the Wnt signaling pathway. PCP is associated with somatic BRAF p.V600E mutations activating the MAPK signaling pathway. Understanding their molecular differences is crucial for diagnosis and treatment. This study aimed to analyze common somatic alterations in ACP and PCP using bulk transcriptome sequencing and in situ spatial transcriptomics. RNA sequencing and high-resolution spatial profiling were used to detect mutations and examine gene expression differences among ACP, PCP, and healthy pituitary tissue. Whole transcriptome sequencing was performed on 24 tumor samples, with healthy pituitary data from the GTEx portal. Bioinformatics analysis utilized the CTAT mutation pipeline, with Sanger sequencing for validation. Results confirmed BRAF p.V600E mutations in all PCP samples and CTNNB1 mutations in all ACP samples. Differential gene expression analysis highlighted distinct molecular profiles and reinforced the involvement of Wnt and MAPK signaling. Spatial profiling identified 41 differentially expressed genes between ACP and PCP. This study provides critical insights into CP biology, supporting improved diagnostics and potential therapeutic strategies.

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来源期刊
Brain Tumor Pathology
Brain Tumor Pathology 医学-病理学
CiteScore
5.40
自引率
9.10%
发文量
30
审稿时长
>12 weeks
期刊介绍: Brain Tumor Pathology is the official journal of the Japan Society of Brain Tumor Pathology. This international journal documents the latest research and topical debate in all clinical and experimental fields relating to brain tumors, especially brain tumor pathology. The journal has been published since 1983 and has been recognized worldwide as a unique journal of high quality. The journal welcomes the submission of manuscripts from any country. Membership in the society is not a prerequisite for submission. The journal publishes original articles, case reports, rapid short communications, instructional lectures, review articles, letters to the editor, and topics.Review articles and Topics may be recommended at the annual meeting of the Japan Society of Brain Tumor Pathology. All contributions should be aimed at promoting international scientific collaboration.
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