亨廷顿病的不对称脑萎缩:一项死后MRI研究。

IF 2.1 Q3 NEUROSCIENCES
Eardi Lila, David Hunt, Daniel D Child, Caitlin Latimer, Bianca Le, Marie Davis, Suman Jayadev, Thomas D Bird, Ali Shojaie, Christine L Mac Donald
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引用次数: 0

摘要

背景:亨廷顿氏病是一种由HTT基因CAG重复扩增引起的进行性常染色体显性神经退行性疾病。纹状体的中棘神经元特别容易受到疾病的影响,尾状核和壳核的萎缩可以在症状出现前几年通过神经影像学记录下来。目的在本研究中,我们旨在表征亨廷顿病患者和对照组之间特定区域的灰质和白质差异。方法对15例诊断为症状性亨廷顿病的成年人和26例对照者进行了尸检MRI研究,目的是比较两组之间区域灰质和白质体积的差异。结果研究显示亨廷顿舞蹈病患者的灰质和白质体积减少,尾状核和壳核的影响最大。值得注意的是,萎缩主要发生在左半球,特别是影响到脑包皮部、中央前、边缘上和眶回部附近的灰质和白质区域,以及眶额外侧皮层。在对照组中,不对称源于左半球区域比右半球区域大,而在亨廷顿病组中观察到相反的模式。结论亨廷顿舞蹈病发生进行性、弥漫性和不对称的灰质和白质萎缩。这种不对称的原因尚不清楚;然而,我们的研究提供了先前报道的亨廷顿病灰质和白质变化的更详细的特征,通过死后组织病理学和MRI研究观察到。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Asymmetric brain atrophy in Huntington's disease: A postmortem MRI study.

BackgroundHuntington's disease is a progressive, autosomal dominant, neurodegenerative disease caused by a CAG repeat expansion in the HTT gene. Medium spiny neurons of the striatum are especially vulnerable to the disease, and atrophy of the caudate and putamen can be documented by neuroimaging years before the onset of symptoms.ObjectiveIn this study, we aimed to characterize region-specific gray and white matter differences between Huntington's disease patients and controls.MethodsWe conducted a postmortem MRI study of the brains of 15 adults diagnosed with symptomatic Huntington's disease and 26 control subjects, aiming to compare the differences in regional grey and white matter volumes between the two groups.ResultsThe study revealed decreased volumes in both grey and white matter in patients with Huntington's disease, with the largest effect sizes observed in caudate and putamen. Notably, the atrophy predominantly affected the left hemisphere, particularly impacting grey and white matter regions adjacent to the pars opercularis, precentral, supramarginal, and pars orbitalis gyri, and the lateral orbitofrontal cortex. In the control group, asymmetry stems from larger left hemisphere regions compared to right, whereas an opposite pattern is observed in the Huntington's disease group.ConclusionsThese results suggest progressive, diffuse, and asymmetric grey and white matter atrophy occurs in Huntington's disease. The reasons for this asymmetry remain unknown; however, our study provides a more detailed characterization of previously reported grey and white matter changes in Huntington's disease, as observed through postmortem histopathological and MRI studies.

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来源期刊
CiteScore
4.80
自引率
9.70%
发文量
60
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