杜氏肌营养不良症的完全个性化建模。

IF 3.7 3区 综合性期刊 Q1 MULTIDISCIPLINARY SCIENCES
Victor Applebaum, Evan Baker, Thomas Kim, Georgia Stimpson, Peter Challenor, Kyle Carlton Abesser Wedgwood, Matthew Anderson, Ian Bamsey, Giovanni Baranello, Adnan Manzur, Francesco Muntoni, Krasimira Tsaneva-Atanasova
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引用次数: 0

摘要

杜氏肌营养不良症是一种进行性神经肌肉疾病,其特征是肌肉逐渐减弱和恶化,导致患者失去行动能力。这种活动能力的下降可以使用北极星动态评估(NSAA)分数,以及10米步行时间和从地板上站起来所需的时间等措施来有效评估。我们提出了一个动态线性模型来预测这些临床结果的轨迹,主要关注NSAA评分。我们的模型旨在帮助临床医生预测疾病的进展,从而为患者提供更明智和个性化的治疗计划。我们还评估了我们的模型在生成合成NSAA分数数据集方面的有效性。我们评估了我们的建模方法的性能,并将结果与以前的研究结果进行了比较。我们发现,最稳健的模型显示更窄的预测区间和改进的分位数覆盖,表明更高的预测精度和可靠性。本文是主题问题“医疗保健和生物系统的不确定性量化(第2部分)”的一部分。
本文章由计算机程序翻译,如有差异,请以英文原文为准。

Fully personalized modelling of Duchenne Muscular Dystrophy ambulation.

Fully personalized modelling of Duchenne Muscular Dystrophy ambulation.

Fully personalized modelling of Duchenne Muscular Dystrophy ambulation.

Duchenne Muscular Dystrophy is a progressive neuromuscular disorder characterized by the gradual weakening and deterioration of muscles, leading to loss of ambulation in affected individuals. This decline in mobility can be effectively assessed using the North Star Ambulatory Assessment (NSAA) scores, along with measures such as the 10-m walk time and the time taken to rise from the floor. We propose a dynamic linear model to predict the trajectories of these clinical outcomes, with a primary focus on NSAA scores. Our model aims to assist clinicians in forecasting the progression of the disease, thereby enabling more informed and personalized treatment plans for their patients. We also evaluate the effectiveness of our models in generating synthetic NSAA score datasets. We assess the performance of our modelling approach and compare the results with those of a previous study. We show that the most robust model demonstrates narrower prediction intervals and improved quantile coverage, indicating superior predictive accuracy and reliability.This article is part of the theme issue 'Uncertainty quantification for healthcare and biological systems (Part 2)'.

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来源期刊
CiteScore
9.30
自引率
2.00%
发文量
367
审稿时长
3 months
期刊介绍: Continuing its long history of influential scientific publishing, Philosophical Transactions A publishes high-quality theme issues on topics of current importance and general interest within the physical, mathematical and engineering sciences, guest-edited by leading authorities and comprising new research, reviews and opinions from prominent researchers.
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