MEIS1::NCOA1原发性肾梭形细胞肉瘤:7例独特临床病理实体报告

IF 4.5 1区 医学 Q1 PATHOLOGY
American Journal of Surgical Pathology Pub Date : 2025-06-01 Epub Date: 2025-03-31 DOI:10.1097/PAS.0000000000002386
Pedram Argani, Sintawat Wangsiricharoen, Maria Tretiakova, Yajuan J Liu, Sara M Falzarano, Katrina Collins, Fadi Brimo, John M Gross, Ezra Baraban, Andres Matoso, Kristina Wakeman, Christopher Corless, Tanaya Neff, Benjamin F Smith, Ali Abdel Satir, Abbas Agaimy, Cristina R Antonescu, Gregory W Charville, Ankur R Sangoi
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引用次数: 0

摘要

包含MEIS1::NCOA2基因融合的原始肉瘤最初于2018年在肾脏中被描述,随后在其他器官中被报道。这些变细胞肿瘤的特征是单形原始丰满的梭形细胞形成结节和螺旋,以及难以描述的束状、实状和故事状模式。与具有相同基因融合的主要骨内横纹肌肉瘤相比,它们缺乏骨骼肌分化。我们描述了7例新的原发性原发性肾肉瘤与MEIS1::NCOA1基因融合。虽然它们的形态与MEIS1::NCOA2肾肉瘤有重叠,但7例中有3例含有脂肪组织。大多数囊性上皮元件紧密混合,对雌激素受体表现出斑片状免疫反应,对WT1蛋白表现出核标记,导致4例恶性混合上皮间质瘤(MEST)和1例后肾间质瘤的鉴别诊断。肿瘤表现出广泛的临床病理特征,从诊断后9年转移的温和的低级别肿瘤到多次复发的高级别肉瘤,最终导致患者在1年内死亡。综上所述,MEIS1::NCOA1原发肉瘤与先前描述的MEIS1::NCOA2原发肾肉瘤重叠,代表了一种独特的肾脏肿瘤,可被误认为恶性MEST。分级从低到高,但即使是低分级的肿瘤也需要长期的临床随访。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
MEIS1::NCOA1 Primitive Spindle Cell Sarcoma of the Kidney : Report of 7 Cases of a Distinctive Clinicopathologic Entity.

Primitive sarcomas harboring the MEIS1::NCOA2 gene fusion were originally described in the kidney in 2018, and subsequently reported in other organs. These variably cellular neoplasms feature monomorphic primitive plump spindle cells forming nodules and whorls in addition to nondescript fascicular, solid, and storiform patterns. They lack skeletal muscle differentiation in contrast to the primarily intraosseous rhabdomyosarcomas that harbor the same gene fusion. We describe 7 new primary primitive renal sarcomas with MEIS1::NCOA1 gene fusions. Although their morphology overlaps with that described in MEIS1::NCOA2 renal sarcoma, 3 of the 7 cases contained adipose tissue. The majority had intimately admixed entrapped cystic epithelial elements and demonstrated patchy immunoreactivity for estrogen receptor and nuclear labeling for WT1 protein, leading to the differential diagnosis of malignant mixed epithelial stromal tumor (MEST) in 4 cases and metanephric stromal tumor in one. The neoplasms demonstrate a broad spectrum of clinicopathologic features ranging from a bland low-grade neoplasm that metastasized 9 years after diagnosis to a high-grade sarcoma with multiple recurrences, ultimately leading to patient death in under 1 year. In summary, MEIS1::NCOA1 primitive sarcomas overlap with the previously described MEIS1::NCOA2 primitive renal sarcomas and represent a distinctive renal neoplasm that can be mistaken for malignant MEST. Grade ranges from low to high but even low-grade neoplasms require long-term clinical follow-up.

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来源期刊
CiteScore
10.30
自引率
5.40%
发文量
295
审稿时长
1 months
期刊介绍: The American Journal of Surgical Pathology has achieved worldwide recognition for its outstanding coverage of the state of the art in human surgical pathology. In each monthly issue, experts present original articles, review articles, detailed case reports, and special features, enhanced by superb illustrations. Coverage encompasses technical methods, diagnostic aids, and frozen-section diagnosis, in addition to detailed pathologic studies of a wide range of disease entities. Official Journal of The Arthur Purdy Stout Society of Surgical Pathologists and The Gastrointestinal Pathology Society.
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