遗传性代谢性癫痫患儿的神经影像学研究。

IF 7.7 1区 医学 Q1 CLINICAL NEUROLOGY
Neurology Pub Date : 2025-04-22 Epub Date: 2025-03-25 DOI:10.1212/WNL.0000000000213485
Itay Tokatly Latzer, Edward Yang, Vitor Lauar Pimenta de Figueiredo, Susie Y Huang, Teppei Matsubara, Phillip L Pearl
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引用次数: 0

摘要

遗传性代谢性癫痫(IMEs)是一种遗传性代谢性疾病,其中癫痫发作类型多样,通常难治性,是总体结果的主要表现和主要决定因素之一。在任何因不明原因引起的难治性癫痫病例中,应怀疑代谢病因。虽然个体ime的发生率很少见,但其累积患病率足以构成重大的临床挑战。与遗传和代谢测试同时,神经影像学被认为是他们调查的第一层的一部分,目的是确认或反对表型。它可能是正常的或非特异性的;然而,正如本综述所述,有相当数量的ime与不同的MRI或磁共振波谱模式相关。除了缩小或支持他们的诊断,这些神经成像模式可以作为监测治疗效果和结果的生物标志物。其他先进的模式和技术,如PET, fMRI,弥散张量成像,MRI g-ratio制图和功能近红外光谱,拓宽了我们对其病理生理学,临床过程,靶向治疗开发和预后的见解。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Neuroimaging in Children With Inherited Metabolic Epilepsies.

Inherited metabolic epilepsies (IMEs) represent inherited metabolic disorders in which seizures, various in types and typically intractable, are one of the predominant manifestations and primary determinants of the overall outcome. A metabolic etiology should be suspected in any case of refractory seizures stemming from an undetermined cause. While the occurrence rate of individual IMEs is rare, their cumulative prevalence is high enough to pose a significant clinical challenge. Concurrently with genetic and metabolic tests, neuroimaging is considered part of the first tier of their investigation, attained with an aim to affirm or counter the phenotype. It may be normal or nonspecific; however, as described by this overview, there is an appreciable number of IMEs associated with distinct MRI or magnetic resonance spectroscopy patterns. Apart from narrowing or supporting their diagnoses, these neuroimaging patterns may serve as biomarkers to monitor treatment efficacy and outcome. Other advanced modalities and techniques, such as PET, fMRI, diffusion tensor imaging, MRI g-ratio mapping, and functional near-infrared spectroscopy, broaden our insights relating to their pathophysiology, clinical course, targeted treatment development, and prognosis.

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来源期刊
Neurology
Neurology 医学-临床神经学
CiteScore
12.20
自引率
4.00%
发文量
1973
审稿时长
2-3 weeks
期刊介绍: Neurology, the official journal of the American Academy of Neurology, aspires to be the premier peer-reviewed journal for clinical neurology research. Its mission is to publish exceptional peer-reviewed original research articles, editorials, and reviews to improve patient care, education, clinical research, and professionalism in neurology. As the leading clinical neurology journal worldwide, Neurology targets physicians specializing in nervous system diseases and conditions. It aims to advance the field by presenting new basic and clinical research that influences neurological practice. The journal is a leading source of cutting-edge, peer-reviewed information for the neurology community worldwide. Editorial content includes Research, Clinical/Scientific Notes, Views, Historical Neurology, NeuroImages, Humanities, Letters, and position papers from the American Academy of Neurology. The online version is considered the definitive version, encompassing all available content. Neurology is indexed in prestigious databases such as MEDLINE/PubMed, Embase, Scopus, Biological Abstracts®, PsycINFO®, Current Contents®, Web of Science®, CrossRef, and Google Scholar.
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