Maria Riedmeier, Jan Idkowiak, Heidi Frey, Sonir R R Antonini, Gabriela Fernandes Luiz Canali, Carl Friedrich Classen, Nerea Domínguez-Pinilla, Martin Fassnacht, Steffen Fuchs, Christoph Härtel, Dominika Janús, Ronald de Krijger, Tezer Kutluk, Ngoc Lan Bui, Jagdish Prasad Meena, Mouna Mezoued, Jessica Munarin, Max M van Noesel, Nihal Özdemir Köse, Simon H Pearce, Thomas Perwein, Soraya Puglisi, Jaydira Del Rivero, Paul G Schlegel, Irene Schmid, Gerdi Tuli, Justyna Walenciak, Bilgehan Yalcin, Verena Wiegering
{"title":"儿童肾上腺皮质癌的炎症评分。","authors":"Maria Riedmeier, Jan Idkowiak, Heidi Frey, Sonir R R Antonini, Gabriela Fernandes Luiz Canali, Carl Friedrich Classen, Nerea Domínguez-Pinilla, Martin Fassnacht, Steffen Fuchs, Christoph Härtel, Dominika Janús, Ronald de Krijger, Tezer Kutluk, Ngoc Lan Bui, Jagdish Prasad Meena, Mouna Mezoued, Jessica Munarin, Max M van Noesel, Nihal Özdemir Köse, Simon H Pearce, Thomas Perwein, Soraya Puglisi, Jaydira Del Rivero, Paul G Schlegel, Irene Schmid, Gerdi Tuli, Justyna Walenciak, Bilgehan Yalcin, Verena Wiegering","doi":"10.1530/ERC-24-0244","DOIUrl":null,"url":null,"abstract":"<p><p>Inflammation-based scores have been demonstrated to be independent prognostic factors in predicting outcomes in adult adrenocortical carcinoma (ACC). We aimed to investigate the prognostic role of these scores in pediatric adrenocortical carcinoma (pACC) patients. An international multicenter analysis was conducted on a pediatric cohort from 21 ACC centers. Pretreatment inflammation-based scoring parameters, including neutrophil-to-lymphocyte ratio (NLR), derived neutrophil-to-lymphocyte ratio (dNLR), platelet-to-lymphocyte ratio (PLR), monocyte-to-lymphocyte ratio (MLR) and serum albumin, as well as clinical parameters, were analyzed. The primary endpoint was 10-year overall survival (OS). One hundred twenty-nine pediatric patients (50.4% females, mean age 87 months) across all tumor stages with a median follow-up of 36 months were included. 107/108 patients underwent primary surgery, and 62/106 received systemic treatment at the time of diagnosis. Of 102 patients, 27 died from disease. In the univariable analysis, NLR ≥5 (HR 8.0, 95% CI 3.4-19.1), MLR ≥0.28 (HR 4.2, 95% CI 1.7-10.4), PLR ≥190 (HR 4.5, 95% CI 2.0-10.4) and dNLR ≥1.44 (HR 5.9, 95% CI 2.3-15.5), as well as clinical parameters age ≥4 years (HR 5.5, 95% CI 1.9-15.8), tumor stage IV (HR 5.7, 95% CI 2.7-11.9) and incomplete resection status (HR 8.0, 95% CI 3.6-17.7) were significantly associated with reduced 10-year OS. After multivariable adjustment, only tumor stage IV (HR 336.7, 95% CI 5.8-19,518.1) and MLR ≥0.28 (HR 247.1, 95% CI = 3.1-19,907.5) were significantly associated with an unfavorable outcome. Inflammation-based scores tend to have prognostic value in pACC and could serve as prognostic tools after further validation in future studies with sufficient case numbers.</p>","PeriodicalId":93989,"journal":{"name":"Endocrine-related cancer","volume":" ","pages":""},"PeriodicalIF":0.0000,"publicationDate":"2025-03-28","publicationTypes":"Journal Article","fieldsOfStudy":null,"isOpenAccess":false,"openAccessPdf":"https://www.ncbi.nlm.nih.gov/pmc/articles/PMC12002726/pdf/","citationCount":"0","resultStr":"{\"title\":\"Inflammation-based score in pediatric adrenocortical carcinoma.\",\"authors\":\"Maria Riedmeier, Jan Idkowiak, Heidi Frey, Sonir R R Antonini, Gabriela Fernandes Luiz Canali, Carl Friedrich Classen, Nerea Domínguez-Pinilla, Martin Fassnacht, Steffen Fuchs, Christoph Härtel, Dominika Janús, Ronald de Krijger, Tezer Kutluk, Ngoc Lan Bui, Jagdish Prasad Meena, Mouna Mezoued, Jessica Munarin, Max M van Noesel, Nihal Özdemir Köse, Simon H Pearce, Thomas Perwein, Soraya Puglisi, Jaydira Del Rivero, Paul G Schlegel, Irene Schmid, Gerdi Tuli, Justyna Walenciak, Bilgehan Yalcin, Verena Wiegering\",\"doi\":\"10.1530/ERC-24-0244\",\"DOIUrl\":null,\"url\":null,\"abstract\":\"<p><p>Inflammation-based scores have been demonstrated to be independent prognostic factors in predicting outcomes in adult adrenocortical carcinoma (ACC). 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In the univariable analysis, NLR ≥5 (HR 8.0, 95% CI 3.4-19.1), MLR ≥0.28 (HR 4.2, 95% CI 1.7-10.4), PLR ≥190 (HR 4.5, 95% CI 2.0-10.4) and dNLR ≥1.44 (HR 5.9, 95% CI 2.3-15.5), as well as clinical parameters age ≥4 years (HR 5.5, 95% CI 1.9-15.8), tumor stage IV (HR 5.7, 95% CI 2.7-11.9) and incomplete resection status (HR 8.0, 95% CI 3.6-17.7) were significantly associated with reduced 10-year OS. After multivariable adjustment, only tumor stage IV (HR 336.7, 95% CI 5.8-19,518.1) and MLR ≥0.28 (HR 247.1, 95% CI = 3.1-19,907.5) were significantly associated with an unfavorable outcome. 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引用次数: 0
摘要
基于炎症的评分已被证明是预测成人ACC预后的独立预后因素。我们的目的是研究这些评分在pACC患者中的预后作用。对来自21个ACC中心的儿童队列进行了一项国际多中心分析。分析预处理炎症评分参数,包括中性粒细胞与淋巴细胞比值(NLR)、衍生中性粒细胞与淋巴细胞比值(dNLR)、血小板与淋巴细胞比值(PLR)、单核细胞与淋巴细胞比值(MLR)、血清白蛋白及临床参数。主要终点为10年总生存期(OS)。129名儿童患者(50.4%为女性,平均年龄87个月)跨越所有肿瘤分期,中位随访时间为36个月。107/108例患者在诊断时接受了初始手术,62/106例接受了全身治疗。102名患者中,27人死于疾病。在单变量分析中,NLR≥5 (HR 8.0, 95% CI 3.4-19.1), MLR≥0.28 (HR 4.2, 95% CI 1.7-10.4), PLR≥190 (HR 4.5, 95% CI 2.0-10.4), dNLR≥1.44 (HR 5.9, 95% CI 2.3-15.5),以及临床参数年龄≥4岁(HR 5.5;95% CI 1.9-15.8),肿瘤IV期(HR 5.7, 95% CI 2.7-11.9)和不完全切除状态(HR 8.0, 95% CI 3.6-17.7)与10年OS降低显著相关。多变量调整后,只有IV期肿瘤(HR 336.7, 95% CI= 5.8-19518.1)和MLR≥0.28 (HR 247.1, 95% CI=3.1-19907.5)与不良结局显著相关。基于炎症的评分在pACC中往往具有预后价值,在未来有足够病例数的研究中进一步验证后,可以作为预后工具。
Inflammation-based score in pediatric adrenocortical carcinoma.
Inflammation-based scores have been demonstrated to be independent prognostic factors in predicting outcomes in adult adrenocortical carcinoma (ACC). We aimed to investigate the prognostic role of these scores in pediatric adrenocortical carcinoma (pACC) patients. An international multicenter analysis was conducted on a pediatric cohort from 21 ACC centers. Pretreatment inflammation-based scoring parameters, including neutrophil-to-lymphocyte ratio (NLR), derived neutrophil-to-lymphocyte ratio (dNLR), platelet-to-lymphocyte ratio (PLR), monocyte-to-lymphocyte ratio (MLR) and serum albumin, as well as clinical parameters, were analyzed. The primary endpoint was 10-year overall survival (OS). One hundred twenty-nine pediatric patients (50.4% females, mean age 87 months) across all tumor stages with a median follow-up of 36 months were included. 107/108 patients underwent primary surgery, and 62/106 received systemic treatment at the time of diagnosis. Of 102 patients, 27 died from disease. In the univariable analysis, NLR ≥5 (HR 8.0, 95% CI 3.4-19.1), MLR ≥0.28 (HR 4.2, 95% CI 1.7-10.4), PLR ≥190 (HR 4.5, 95% CI 2.0-10.4) and dNLR ≥1.44 (HR 5.9, 95% CI 2.3-15.5), as well as clinical parameters age ≥4 years (HR 5.5, 95% CI 1.9-15.8), tumor stage IV (HR 5.7, 95% CI 2.7-11.9) and incomplete resection status (HR 8.0, 95% CI 3.6-17.7) were significantly associated with reduced 10-year OS. After multivariable adjustment, only tumor stage IV (HR 336.7, 95% CI 5.8-19,518.1) and MLR ≥0.28 (HR 247.1, 95% CI = 3.1-19,907.5) were significantly associated with an unfavorable outcome. Inflammation-based scores tend to have prognostic value in pACC and could serve as prognostic tools after further validation in future studies with sufficient case numbers.