新生儿镰状细胞病筛查:葡萄牙人口试点研究结果

IF 4 Q1 GENETICS & HEREDITY
Diogo Rodrigues, Ana Marcão, Lurdes Lopes, Ana Ventura, Teresa Faria, Anabela Ferrão, Carolina Gonçalves, Paula Kjöllerström, Ana Castro, Sofia Fraga, Marta Almeida, Tabita Maia, João Gomes, Ana Lachado, Isabel Guerra, Fátima Ferreira, Fernanda Trigo, Celeste Bento, Laura Vilarinho
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引用次数: 0

摘要

葡萄牙新生儿筛查方案目前包括28种疾病:先天性甲状腺功能减退症、囊性纤维化、24种先天性代谢缺陷、镰状细胞病和脊髓性肌萎缩症。这项镰状细胞病新生儿筛查的试点研究于2021年5月至2023年12月期间进行,包括188,217份样本,其中第一阶段在里斯本和塞图巴尔地区,包括24,130名新生儿,第二阶段在全国,包括164,087名新生儿。采用毛细管电泳对DBS样品进行分析。在I期研究中,通过鉴定24例HbSS和2例HbSC患者,发现镰状细胞病的高出生发生率(1:928 NBs)。当镰状细胞病新生儿筛查的试点研究扩大到全国水平时,这一出生发病率有所下降,但仍然很重要,共发现67例镰状细胞病患者(59例HbSS和8例HbSC),显示出生发病率为1:2449 NBs。这些数据表明,镰状细胞病在葡萄牙变得越来越重要,从而反映了欧洲的总体趋势,即镰状细胞病已经被认为是一个公共卫生问题。因此,它强调了其在2024年1月纳入葡萄牙国家新生儿筛查计划小组的重要性,从而允许这些患者的早期识别和临床随访。
本文章由计算机程序翻译,如有差异,请以英文原文为准。

Newborn Screening for Sickle Cell Disease: Results from a Pilot Study in the Portuguese Population.

Newborn Screening for Sickle Cell Disease: Results from a Pilot Study in the Portuguese Population.

The Portuguese Newborn Screening Program currently includes 28 pathologies: congenital hypothyroidism, cystic fibrosis, 24 inborn errors of metabolism, sickle cell disease and spinal muscular atrophy. This pilot study for sickle cell disease newborn screening, including 188,217 samples, was performed between May 2021 and December 2023, with phase I, including 24,130 newborns, in the Lisbon and Setubal districts and phase II, including 164,087 newborns, in the whole country. DBS samples were analyzed through capillary electrophoresis. In phase I, a high birth incidence of sickle cell disease was found (1:928 NBs), resulting from the identification of 24 HbSS and 2 HbSC patients. This birth incidence decreased but remained significant when the pilot study for sickle cell disease newborn screening was expanded to a national level, with the identification of 67 sickle cell disease patients (59 HbSS and 8 HbSC), revealing a birth incidence of 1:2449 NBs. These data suggest that this condition is becoming increasingly relevant in Portugal, thus reflecting a general European trend, where sickle cell disease is already recognized as a public health problem. Therefore, it highlights the importance of its integration into the Portuguese National Newborn Screening Program panel in January 2024, thus allowing the early identification and clinical follow-up of these patients.

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来源期刊
International Journal of Neonatal Screening
International Journal of Neonatal Screening Medicine-Pediatrics, Perinatology and Child Health
CiteScore
6.70
自引率
20.00%
发文量
56
审稿时长
11 weeks
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