法布里病对心脏的影响:最新进展、未解决的问题和未满足的需求。

IF 1.7 4区 医学 Q3 CARDIAC & CARDIOVASCULAR SYSTEMS
European Heart Journal Supplements Pub Date : 2025-02-19 eCollection Date: 2025-02-01 DOI:10.1093/eurheartjsupp/suae104
Maurizio Pieroni, Chiara Zocchi, Michele Ciabatti
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引用次数: 0

摘要

法布里病是一种由α-半乳糖苷酶A活性不足引起的x连锁溶酶体贮积障碍,导致球三烷基神经酰胺在包括心脏在内的各种组织中积累。累及心脏是法布里病的一个显著特征,也是其发病率和死亡率的主要原因,表现为左心室肥厚、心肌缺血、心力衰竭和心律失常。次级机制,由溶酶体储存触发,有助于心肌损伤,特别是心肌炎症。早期心脏受累可能是微妙的,但随着疾病的进展,它成为发病率和死亡率的主要决定因素。诊断技术的最新进展,如具有T1和T2定位的先进心脏磁共振成像,改善了fabry相关心脏病的早期检测。酶替代疗法和较新的治疗方法,如伴侣疗法,在早期开始时已显示出控制心脏表现的潜力,而在病程晚期诊断的患者中,心脏受累的进展可能难以停止。基因治疗和底物减少治疗是新兴的治疗方式,有希望,但需要进一步的临床评估。现有治疗方法的有限疗效和心脏对治疗反应的可变性是主要未解决的问题,此外还有监测疾病进展方面的挑战,以及需要针对次要机制的额外治疗策略。临床实践中未满足的需求包括确定疾病特异性和心脏特异性生物标志物,用于早期检测、分期和监测心脏损伤。同样,预后分层和更好地预防心血管并发症的策略对于改善这些患者的护理至关重要。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Cardiac involvement in Fabry disease: Recent advances, unresolved issues, and unmet needs.

Fabry disease is an X-linked lysosomal storage disorder caused by deficient activity of the enzyme α-galactosidase A, leading to the accumulation of globotriaosylceramide in various tissues, including the heart. Cardiac involvement is a prominent feature and a major cause of morbidity and mortality in Fabry disease, manifesting as left ventricular hypertrophy, myocardial ischaemia, heart failure, and arrhythmias. Secondary mechanisms, triggered by lysosomal storage, contribute to myocardial damage, in particular, myocardial inflammation. Early cardiac involvement can be subtle, but with disease progression, it becomes a major determinant of morbidity and mortality. Recent progresses in diagnostic techniques, such as advanced cardiac magnetic resonance imaging with T1 and T2 mapping, have improved early detection of Fabry-related cardiac disease. Enzyme replacement therapy and newer treatments like chaperone therapy have shown potential in managing cardiac manifestations when initiated early, while the progression of cardiac involvement may be difficult to halt in patients diagnosed late in the disease course. Gene therapy and substrate reduction therapy are emerging treatment modalities that hold promise but require further clinical evaluation. The limited efficacy of available therapies and the variability of cardiac response to treatment represent main unresolved issues, together with challenges in monitoring disease progression, and the need for additional therapeutic strategies targeting secondary mechanisms. Unmet needs in clinical practice include the identification of disease-specific and cardiac-specific biomarkers for early detection, staging, and monitoring cardiac damage. Similarly, strategies for prognostic stratification and better prevention of cardiovascular complications are essential to improve the care of these patients.

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来源期刊
European Heart Journal Supplements
European Heart Journal Supplements 医学-心血管系统
CiteScore
3.00
自引率
0.00%
发文量
575
审稿时长
12 months
期刊介绍: The European Heart Journal Supplements (EHJs) is a long standing member of the ESC Journal Family that serves as a publication medium for supplemental issues of the flagship European Heart Journal. Traditionally EHJs published a broad range of articles from symposia to special issues on specific topics of interest. The Editor-in-Chief, Professor Roberto Ferrari, together with his team of eminent Associate Editors: Professor Francisco Fernández-Avilés, Professors Jeroen Bax, Michael Böhm, Frank Ruschitzka, and Thomas Lüscher from the European Heart Journal, has implemented a change of focus for the journal. This entirely refreshed version of the European Heart Journal Supplements now bears the subtitle the Heart of the Matter to give recognition to the focus the journal now has. The EHJs – the Heart of the Matter intends to offer a dedicated, scientific space for the ESC, Institutions, National and Affiliate Societies, Associations, Working Groups and Councils to disseminate their important successes globally.
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