calr突变骨髓增生性肿瘤:来自下一代测序的见解。

IF 2 3区 生物学 Q3 BIOTECHNOLOGY & APPLIED MICROBIOLOGY
Aleksandra Mroczkowska-Bękarciak, Agnieszka Szeremet, Olga Chyrko, Tomasz Wróbel
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引用次数: 0

摘要

原发性血小板增多症和原发性骨髓纤维化属于BCR:: abl1阴性骨髓增生性肿瘤。JAK2、CALR和MPL基因突变的存在对于骨髓增生性肿瘤的诊断至关重要。这些突变被称为“驱动”突变。然而,不仅在MPN患者中发现了先导突变,而且在半数以上的原发性血小板增多症患者和80%以上的骨髓纤维化患者中也发现了附加突变。新一代测序技术使发现预后、预测和诊断指标成为可能。共存的突变与治疗反应降低、总生存期缩短以及转化为急性髓性白血病或骨髓纤维化的高风险相关。研究组由42例诊断为BCR:: abl1阴性MPN且存在CALR基因突变的患者组成。研究资料为档案资料,DNA取自患者外周血。40个基因(17个基因,23个热点)测序使用商业试剂盒AmpliSeq for Illumina Myeloid Panel应用靶向下一代测序方法。本研究使用Illumina MiniSeq平台。利用生物信息学工具和遗传数据库对获得的遗传结果进行分析。我们研究了42例calr阳性ET (n = 28)和MF (n = 14)患者的NGS面板检测。整个患者诊断时的中位年龄为58岁。在整个队列中,48%的患者检测到额外的突变。研究人群中最常见的突变基因是ASXL1、TET2和DNMT3A,这些基因在很大程度上与表观遗传调控机制有关。NGS小组研究在CALR突变mpn的诊断和预后评估方面取得了突破。进行这种全面研究的能力提供了有关疾病生物学和选择适当治疗方案的宝贵信息。新技术的使用表明,不仅驱动突变对患者有临床意义。NGS有可能提高诊断和预后的准确性和有效性。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
CALR-mutant myeloproliferative neoplasms: insights from next-generation sequencing.

Essential thrombocythemia and primary myelofibrosis belong to the group of BCR::ABL1-negative myeloproliferative neoplasms. The presence of mutations in the JAK2, CALR, and MPL genes is essential for the diagnosis of myeloproliferative neoplasms. These mutations are called "driver" mutations. However, not only leading mutations have been identified in patients with MPN, but also more than half of individuals with essential thrombocythemia and more than 80% of patients with myelofibrosis have additional mutations. One technique that makes it possible to find prognostic, predictive, and diagnostic indicators is next-generation sequencing. Coexisting mutations are associated with reduced response to therapy, shortened overall survival, and a higher risk of transformation to acute myeloid leukemia or myelofibrosis. The study group consisted of 42 patients with the diagnosis of BCR::ABL1-negative MPN and the presence of a mutation in the CALR gene. The research material was archival, and DNA was obtained from patients' peripheral blood. Forty genes (17 genes, 23 hotspots) were sequenced using the commercial kit AmpliSeq for Illumina Myeloid Panel applying the targeted next-generation sequencing approach. For the study, the Illumina MiniSeq platform was used. The analysis of the obtained genetic results was carried out using bioinformatics tools and genetic databases. We studied 42 CALR-positive ET (n = 28) and MF (n = 14) patients with NGS panel testing. The median age at diagnosis of the entire patient series was 58 years. Additional mutations were detected in 48% of patients in the whole cohort. The most frequently mutated genes in the study population were ASXL1, TET2, and DNMT3A, which are largely associated with epigenetic regulatory mechanisms. NGS panel studies represent a breakthrough in the diagnostic and prognostic evaluation of MPNs with CALR mutations. The ability to perform such a comprehensive study provides valuable information on the biology of the disease and the selection of the appropriate treatment regimen. The use of new technologies shows that not only driver mutations have clinical significance for the patient. NGS has the potential to increase the precision and effectiveness of diagnosis and prognosis.

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来源期刊
Journal of Applied Genetics
Journal of Applied Genetics 生物-生物工程与应用微生物
CiteScore
4.30
自引率
4.20%
发文量
62
审稿时长
6-12 weeks
期刊介绍: The Journal of Applied Genetics is an international journal on genetics and genomics. It publishes peer-reviewed original papers, short communications (including case reports) and review articles focused on the research of applicative aspects of plant, human, animal and microbial genetics and genomics.
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