马凡氏综合征:来自动物模型的见解。

IF 2.8 3区 生物学 Q2 GENETICS & HEREDITY
Frontiers in Genetics Pub Date : 2025-01-06 eCollection Date: 2024-01-01 DOI:10.3389/fgene.2024.1463318
Yuanyuan Jiang, Ping Jia, Xiaoying Feng, Dingding Zhang
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引用次数: 0

摘要

马凡氏综合征(Marfan syndrome, MFS)是一种影响结缔组织的遗传性疾病,主要表现在骨骼、眼睛、心血管系统等。主动脉病变是马凡氏综合征患者死亡的主要原因。纤颤蛋白1基因(FBN1)是参与MFS发病的主要基因。研究表明,MFS的主动脉发病机制与转化生长因子-β (TGF-β)信号通路的失衡有关。然而,MFS的确切分子机制尚不清楚。动物模型可以部分模拟MFS,对MFS的研究至关重要。几种动物已被用于MFS研究,包括鸡、牛、小鼠、猪、斑马鱼、秀丽隐杆线虫和兔子。这些模型是自发或结合基因工程技术开发的。本文就TGF-β信号通路在MFS中的作用及动物模型的潜在应用进行综述,以期为MFS患者提供新的治疗策略。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Marfan syndrome: insights from animal models.

Marfan syndrome (MFS) is an inherited disorder that affects the connective tissues and mainly presents in the bones, eyes, and cardiovascular system, etc. Aortic pathology is the leading cause of death in patients with Marfan syndrome. The fibrillin-1 gene (FBN1) is a major gene involved in the pathogenesis of MFS. It has been shown that the aortic pathogenesis of MFS is associated with the imbalances of the transforming growth factor-beta (TGF-β) signaling pathway. However, the exact molecular mechanism of MFS is unclear. Animal models may partially mimic MFS and are vital to the study of MFS. Several species of animals have been used for MFS studies, including chicks, cattle, mice, pigs, zebrafishes, Caenorhabditis elegans, and rabbits. These models were developed spontaneously or in combination with genetic engineering techniques. This review is to describe the TGF-β signaling pathway in MFS and the potential application of animal models to provide new therapeutic strategies for patients with MFS.

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来源期刊
Frontiers in Genetics
Frontiers in Genetics Biochemistry, Genetics and Molecular Biology-Molecular Medicine
CiteScore
5.50
自引率
8.10%
发文量
3491
审稿时长
14 weeks
期刊介绍: Frontiers in Genetics publishes rigorously peer-reviewed research on genes and genomes relating to all the domains of life, from humans to plants to livestock and other model organisms. Led by an outstanding Editorial Board of the world’s leading experts, this multidisciplinary, open-access journal is at the forefront of communicating cutting-edge research to researchers, academics, clinicians, policy makers and the public. The study of inheritance and the impact of the genome on various biological processes is well documented. However, the majority of discoveries are still to come. A new era is seeing major developments in the function and variability of the genome, the use of genetic and genomic tools and the analysis of the genetic basis of various biological phenomena.
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