哈钦森-吉尔福德早衰综合征:揭示遗传基础、症状和治疗方法的进展。

Therapeutic advances in rare disease Pub Date : 2024-12-16 eCollection Date: 2024-01-01 DOI:10.1177/26330040241305144
Akhil Arun, Athira Rejith Nath, Bonny Thankachan, M K Unnikrishnan
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引用次数: 0

摘要

哈钦森-吉尔福德早衰综合征(HGPS)是一类以加速衰老为特征的罕见遗传疾病,是类早衰综合征的重要模型。本文综述了HGPS的遗传基础、临床表现和并发症。HGPS是由LMNA基因突变引起的,导致产生有缺陷的结构蛋白prelamin a。这种蛋白含有“CAAX”基序,其中C代表半胱氨酸,其异常加工是该疾病病理的核心。HGPS导致多器官系统受到影响,包括心血管、骨骼、神经系统和皮肤系统,造成严重残疾和死亡率增加。心血管问题在HGPS中尤为重要,对制定治疗策略至关重要。治疗方式的最新进展为管理HGPS提供了希望。法尼基转移酶抑制剂和基因干预,如CRISPR-Cas9,已经显示出减轻早衰蛋白相关症状的潜力,在临床前和临床研究中观察到令人鼓舞的结果。此外,雷帕霉素、萝卜硫素和MG132等新兴疗法有望靶向潜在的疾病机制。综合管理方法,包括生长激素治疗,类维生素a和牙科保健,强调提高整体病人的福祉。尽管取得了进展,但需要进一步的研究来揭示类早衰综合征的复杂病理生理机制并开发有效的治疗方法。持续关注解决早衰蛋白积累及其下游效应的治疗对于改善患者护理和HGPS及相关疾病患者的预后至关重要。这篇综述强调了正在进行的了解和对抗类早衰综合征的努力,旨在减轻这些衰弱性疾病带来的负担。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Hutchinson-Gilford progeria syndrome: unraveling the genetic basis, symptoms, and advancements in therapeutic approaches.

Hutchinson-Gilford Progeria syndrome (HGPS) serves as a prominent model for Progeroid syndromes, a group of rare genetic disorders characterized by accelerated aging. This review explores the genetic basis, clinical presentation, and complications of HGPS. HGPS is caused by mutations in the LMNA gene, resulting in the production of a defective structural protein, prelamin A. This protein contains a "CAAX" motif, where C represents cysteine, and its abnormal processing is central to the disease's pathology. HGPS leads to multiple organ systems being affected, including cardiovascular, skeletal, neurological, and dermatological systems, causing severe disability and increased mortality. Cardiovascular issues are particularly significant in HGPS and are crucial for developing therapeutic strategies. Recent advances in treatment modalities offer promise for managing HGPS. Farnesyltransferase inhibitors and genetic interventions, such as CRISPR-Cas9, have shown potential in mitigating progerin-associated symptoms, with encouraging results observed in preclinical and clinical studies. Additionally, emerging therapies such as rapamycin, sulforaphane, and MG132 hold promise in targeting underlying disease mechanisms. Comprehensive management approaches, including growth hormone therapy, retinoids, and dental care, are emphasized to enhance overall patient well-being. Despite progress, further research is essential to unravel the complex pathophysiology of Progeroid syndromes and develop effective treatments. Continued focus on therapies that address progerin accumulation and its downstream effects is vital for improving patient care and outcomes for individuals affected by HGPS and related disorders. This review highlights ongoing efforts to understand and combat Progeroid syndromes, aiming to alleviate the burdens imposed by these debilitating conditions.

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