儿童地中海贫血症:既有方法、老问题、新的非治愈性疗法和治愈前景。

IF 3 3区 医学 Q1 MEDICINE, GENERAL & INTERNAL
Raffaella Origa, Layal Issa
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引用次数: 0

摘要

尽管流行率和发病率有所下降,但地中海贫血症仍是全球公共卫生面临的一项重大挑战。在资源丰富的地区,地中海贫血患儿的预后良好,很有可能在成年和老年时获得良好的生活质量。如果输血治疗管理得当,既能有效缓解无效的红细胞生成及其相关并发症,又能最大限度地减少过量的铁积累,就能实现这一目标。充分的铁螯合作用对于将反应性铁维持在正常范围内至关重要,从而防止因定期输血而不可避免地导致血色素沉着症所造成的器官损伤。对于输血依赖型 beta 地中海贫血症患者来说,新的治疗方法(包括基因治疗等治愈性疗法和红细胞生成调节剂等非治愈性疗法)正在出现。目前已在成人和儿童地中海贫血患者中研究了两种基于基因疗法的治疗方法。第一种方法使用慢病毒来纠正基因缺陷,向患者的细胞提供功能基因拷贝。第二种方法采用 CRISPR/Cas9 基因编辑技术,在分子水平上直接修改缺陷基因。目前还没有非治愈性疗法获准用于儿科。在成人中,唯一可用的药物是 luspatercept,目前正在儿科人群中进行临床试验。然而,在世界许多国家,新的治疗方案仍然是海市蜃楼,甚至输血疗法本身也无法保证大多数患者的治疗效果,而螯合铁疗法的选择则取决于药物的可获得性和可负担性。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Beta Thalassemia in Children: Established Approaches, Old Issues, New Non-Curative Therapies, and Perspectives on Healing.

Despite a decrease in prevalence and incidence rates, beta thalassemia continues to represent a significant public health challenge worldwide. In high-resource settings, children with thalassemia have an open prognosis, with a high chance of reaching adulthood and old age with a good quality of life. This is achievable if transfusion therapy is properly managed, effectively mitigating ineffective erythropoiesis and its associated complications while also minimizing excessive iron accumulation. Adequate iron chelation is essential to maintain reactive forms of iron within the normal range throughout life, thus preventing organ damage caused by hemosiderosis, which inevitably results from a regular transfusion regimen. New therapies, both curative, such as gene therapy, and non-curative, such as modulators of erythropoiesis, are becoming available for patients with transfusion-dependent beta thalassemia. Two curative approaches based on gene therapy have been investigated in both adults and children with thalassemia. The first approach uses a lentivirus to correct the genetic defect, delivering a functional gene copy to the patient's cells. The second approach employs CRISPR/Cas9 gene editing to directly modify the defective gene at the molecular level. No non-curative therapies have received approval for pediatric use. Among adults, the only available drug is luspatercept, which is currently undergoing clinical trials in pediatric populations. However, in many countries around the world, the new therapeutic options remain a mirage, and even transfusion therapy itself is not guaranteed for most patients, while the choice of iron chelation therapy depends on drug availability and affordability.

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来源期刊
Journal of Clinical Medicine
Journal of Clinical Medicine MEDICINE, GENERAL & INTERNAL-
CiteScore
5.70
自引率
7.70%
发文量
6468
审稿时长
16.32 days
期刊介绍: Journal of Clinical Medicine (ISSN 2077-0383), is an international scientific open access journal, providing a platform for advances in health care/clinical practices, the study of direct observation of patients and general medical research. This multi-disciplinary journal is aimed at a wide audience of medical researchers and healthcare professionals. Unique features of this journal: manuscripts regarding original research and ideas will be particularly welcomed.JCM also accepts reviews, communications, and short notes. There is no limit to publication length: our aim is to encourage scientists to publish their experimental and theoretical results in as much detail as possible.
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