不同端粒的不同表型--端粒生物学紊乱和长端粒易患癌症。

IF 5.1 2区 医学 Q1 HEMATOLOGY
Sharon A Savage, Alison A Bertuch
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引用次数: 0

摘要

端粒长度维持和功能所必需的基因中的罕见种系致病变体(GPV)已被认为与两大类人类疾病有关。端粒生物学疾病(TBDs)是一系列威胁生命的疾病,包括骨髓衰竭、肝脏和肺部疾病、癌症以及由端粒维持基因中的 GPV 引起的其他并发症,这些疾病导致端粒变短和/或功能失调以及细胞复制能力下降。与此相反,长端粒癌症易感性(CPLT)是一种与多种癌症风险升高相关的疾病,主要是黑色素瘤、甲状腺癌、肉瘤、胶质瘤和淋巴增殖性肿瘤,其原因是保护蛋白复合基因中的 GPV 导致端粒过度伸长和细胞复制能力增强。虽然端粒是这两种疾病的根源,但 "TBD "一词是用来表达端粒极短或功能失调导致的临床表型及其生物学后果。
本文章由计算机程序翻译,如有差异,请以英文原文为准。
Different phenotypes with different endings-Telomere biology disorders and cancer predisposition with long telomeres.

Rare germline pathogenic variants (GPVs) in genes essential in telomere length maintenance and function have been implicated in two broad classes of human disease. The telomere biology disorders (TBDs) are a spectrum of life-threatening conditions, including bone marrow failure, liver and lung disease, cancer and other complications caused by GPVs in telomere maintenance genes that result in short and/or dysfunctional telomeres and reduced cellular replicative capacity. In contrast, cancer predisposition with long telomeres (CPLT) is a disorder associated with elevated risk of a variety of cancers, primarily melanoma, thyroid cancer, sarcoma, glioma and lymphoproliferative neoplasms caused by GPVs in shelterin complex genes that lead to excessive telomere elongation and increased cellular replicative capacity. While telomeres are at the root of both disorders, the term TBD is used to convey the clinical phenotypes driven by critically short or otherwise dysfunctional telomeres and their biological consequences.

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来源期刊
CiteScore
8.60
自引率
4.60%
发文量
565
审稿时长
1 months
期刊介绍: The British Journal of Haematology publishes original research papers in clinical, laboratory and experimental haematology. The Journal also features annotations, reviews, short reports, images in haematology and Letters to the Editor.
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